NCT04398628

Brief Summary

In parallel with the growth of ATHN's clinical studies, the number of new therapies for all blood disorders is increasing significantly. Some of the recently FDA-approved therapies for congenital and acquired hematologic conditions have not yet demonstrated long-term safety and effectiveness beyond the pivotal trials that led to their approval. In addition, results from well controlled, pivotal studies often cannot be replicated once a therapy has been approved for general use.2,3,4,5 In 2019 alone, the FDA has issued approvals for 24 new therapies for congenital and acquired hematologic conditions.6 In addition, almost 10,000 new studies for hematologic diseases are currently registered on www.clinicaltrials.gov.7 With this increase in potential new therapies possible, it is imperative that clinicians and clinical researchers in the field of non-neoplastic hematology have a uniform, secure, unbiased, and enduring method to collect long-term safety and efficacy data. As emphasized in a recently published review, accurate, uniform and quality national data collection is critical in clinical research, particularly for longitudinal cohort studies covering a lifetime of biologic risk.8

Trial Health

77
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
3,000

participants targeted

Target at P75+ for all trials

Timeline
116mo left

Started Sep 2020

Longer than P75 for all trials

Geographic Reach
1 country

71 active sites

Status
recruiting

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Progress38%
Sep 2020Dec 2035

First Submitted

Initial submission to the registry

May 11, 2020

Completed
10 days until next milestone

First Posted

Study publicly available on registry

May 21, 2020

Completed
4 months until next milestone

Study Start

First participant enrolled

September 30, 2020

Completed
14.7 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

June 1, 2035

Expected
6 months until next milestone

Study Completion

Last participant's last visit for all outcomes

December 1, 2035

Last Updated

January 12, 2026

Status Verified

January 1, 2026

Enrollment Period

14.7 years

First QC Date

May 11, 2020

Last Update Submit

January 9, 2026

Conditions

Outcome Measures

Primary Outcomes (1)

  • To determine the safety of therapies used in the treatment of participants with congenital or acquired non-neoplastic, bleeding and clotting disorders and connective tissue disorders with bleeding tendency (blood disorders).

    Safety will be measured by those events in the European Safety Surveillance (EUHASS)1: 1. Allergic or other acute events 2. Treatment-emergent side effects of therapy 3. Transfusion transmitted infections 4. Inhibitor development 5. Thrombosis 6. Cardiovascular events 7. Malignancies 8. Neurological events 9. Death In addition to the modified EUHASS endpoints, the following events will be collected as adverse events of special interest (AESI): 1. The occurrence of thrombotic microangiopathies, injection site reactions and cases of potential drug-induced liver injury 2. The development of anti-drug antibodies, to be measured and confirmed, if feasible 3. Severe, unanticipated bleeding 4. Hospitalizations 5. Glomerulonephritis 6. Any arm or module-specific AESI as stated in their corresponding Safety Assessment section Additional safety events of interest may be collected.

    15 years

Secondary Outcomes (5)

  • To establish a platform to support study arms and modules for participants with blood disorders.

    15 years

  • To describe medication dosing regimens in participants with blood disorders.

    15 years

  • To describe real-world effectiveness of therapies used for participants with blood disorders.

    15 years

  • To grow and evolve the ATHN Transcends Biorepository for current and future research through the collection of biospecimens from participants enrolled on this protocol

    15 years

  • To describe bleeding events, changes in overall bleeding, and annualized bleeding rate (ABR) as measured by individual bleeding components.

    15 years

Study Arms (7)

Hemophilia

This cohort includes three Arms and six Modules: Previously Untreated Patients (PUPs) Arm Efanestoctocog alfa (ALTUVIIIO®) Module INHIBIT Module Hemophilia Natural History Arm Emicizumab (Hemlibra®) Module Nonacog beta pegol (Rebinyn®)Module Distress Module Hemophilia Gene Therapy Outcomes Arm Etranacogene dezaparvovec (HEMGENIX®) Module

Congenital Platelet Disorders

This cohort includes one Arm and Module: Congenital Platelet Disorders (CPD) Natural History Arm Glanzmann Thrombasthenia (GT) Module

Von Willebrand Disease

No arms or modules

Rare Disorders

No arms or modules

Bleeding NOS

No arms or modules

Thrombosis/Thrombophilia

No arms or modules

Non-Neoplastic Hematologic Conditions

No arms or modules

Eligibility Criteria

Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)
Sampling MethodProbability Sample
Study Population

This is a real-world study in which participants with congenital or acquired blood disorders will be enrolled.

You may not qualify if:

  • Any age
  • Having a congenital or acquired blood disorder; or
  • Having a bleeding phenotype as indicated by an age adjusted abnormal ISTH Bleeding Assessment Tool score with an unknown diagnosis; or
  • Connective tissue disorder with bleeding tendency as indicated by an age adjusted abnormal ISTH Bleeding Assessment Tool score.
  • Eligible for a currently active disease-specific arm.
  • Concurrent enrollment in the ATHNdataset or current ATHNdataset participant.
  • Cohort Participant Selection
  • Each participant is to be enrolled in the cohort for which they qualify as defined below.
  • Hemophilia Cohort
  • Factor VIII or factor IX activity \<50%, without another explanation for low clotting factor other than congenital hemophilia or being a known carrier for congenital hemophilia; OR
  • Carrier for congenital hemophilia with a factor VIII \>=50% or factor IX activity \>=50% with or without a bleeding phenotype as indicated by an ISTH Bleeding Assessment Tool score of ≥4 for adult males, ≥6 for adult females, or ≥3 for children younger than 18 years OR
  • Known congenital hemophilia that have a factor level \>50% after receiving vector, OR 4. Acquired hemophilia.
  • None
  • Von Willebrand Disease Cohort
  • \. Meeting the definition of VWD or low VWF per most recent international guidelines
  • +154 more criteria

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (71)

Arizona Hemophilia and Thrombosis Treatment Center at Phoenix Children's Hospital

Phoenix, Arizona, 85016, United States

RECRUITING

Arkansas Center for Bleeding Disorders

Little Rock, Arkansas, 72202, United States

RECRUITING

Orthopaedic Institute for Children HTC

Los Angeles, California, 90007, United States

RECRUITING

Childrens Hospital Los Angeles

Los Angeles, California, 90027-6016, United States

RECRUITING

UCSF Benioff Children's Hospital Oakland

Oakland, California, 94610, United States

RECRUITING

University of California at Davis Hemophilia Treatment Center

Sacramento, California, 95817, United States

RECRUITING

Loma Linda Hemoglobinopathy and Inherited Bleeding Disorder Program

San Bernardino, California, 92408, United States

RECRUITING

Hemophilia & Thrombosis Treatment Center at UC San Diego Health

San Diego, California, 92121, United States

RECRUITING

Rady Children's Hospital San Diego

San Diego, California, 92123, United States

RECRUITING

University of California, San Francisco Hemophilia & Thrombosis Center

San Francisco, California, 94143, United States

RECRUITING

Connecticut Children's Medical Center

Hartford, Connecticut, 06106, United States

RECRUITING

Yale Hemophilia Treatment Center

New Haven, Connecticut, 06520, United States

RECRUITING

Delaware Hemophilia Treatment Center

Wilmington, Delaware, 19801, United States

RECRUITING

Georgetown University

Washington D.C., District of Columbia, 20007, United States

RECRUITING

Children's National Hemophilia Center

Washington D.C., District of Columbia, 20010, United States

RECRUITING

University of Florida Hemophilia Treatment Center

Gainesville, Florida, 32610, United States

RECRUITING

University of Miami Comprehensive Hemophilia Treatment Center

Miami, Florida, 33136, United States

RECRUITING

Arnold Palmer Hospital for Children - The Haley Center for Children's Cancer and Blood Disorders

Orlando, Florida, 32806, United States

NOT YET RECRUITING

Johns Hopkins All Children's Hospital

St. Petersburg, Florida, 33701, United States

RECRUITING

St. Joseph's Hospital Center for Bleeding & Clotting Disorders

Tampa, Florida, 33607, United States

RECRUITING

Comprehensive Bleeding Disorders Center at Emory University and Children's Healthcare of Atlanta

Atlanta, Georgia, 30308, United States

RECRUITING

Emory/Children's Health Care of Atlanta

Atlanta, Georgia, 30322, United States

RECRUITING

Memorial Health University Medical Center

Savannah, Georgia, 31403, United States

RECRUITING

Rush University Medical Center

Chicago, Illinois, 60612, United States

RECRUITING

Bleeding and Clotting Disorders Institute

Peoria, Illinois, 61664, United States

RECRUITING

Indiana Hemophilia and Thrombosis Center

Indianapolis, Indiana, 46260, United States

RECRUITING

Iowa Hemophilia and Thrombosis Center

Iowa City, Iowa, 52242, United States

RECRUITING

Louisiana Center for Bleeding and Clotting Disorders, Tulane University

New Orleans, Louisiana, 70112, United States

RECRUITING

Maine Hemophilia and Thrombosis Center

Scarborough, Maine, 04074, United States

RECRUITING

Johns Hopkins University Hemophilia Treatment Center

Baltimore, Maryland, 21287, United States

RECRUITING

Massachusetts General Hospital Comprehensive Hemophilia and Thrombosis Treatment Center

Boston, Massachusetts, 02114, United States

NOT YET RECRUITING

Central Michigan Children's Hospital of Michigan

Detroit, Michigan, 48201, United States

RECRUITING

Henry Ford Health System Bleeding and Thrombosis Treatment Center

Detroit, Michigan, 48202, United States

RECRUITING

Mayo Comprehensive Hemophilia Center

Rochester, Minnesota, 55905, United States

RECRUITING

Children's Mercy Hospital - Kansas City

Kansas City, Missouri, 64108, United States

RECRUITING

The John Bouhasin Center for Children with Bleeding Disorders

St Louis, Missouri, 63104, United States

RECRUITING

Cure 4 The Kids Foundation

Las Vegas, Nevada, 89135, United States

RECRUITING

Hemostasis and Thrombosis Center of Nevada

Reno, Nevada, 89509, United States

RECRUITING

Newark Beth Israel Medical Center - Hemophilia Center

Newark, New Jersey, 07122, United States

RECRUITING

University of New Mexico Ted R. Montoya Hemophilia & Thrombosis Program

Albuquerque, New Mexico, 87131, United States

RECRUITING

Western New York BloodCare

Buffalo, New York, 14202, United States

RECRUITING

Northwell Health Hemostasis and Thrombosis Center at Long Island Jewish and Cohen Children's Medical Center

Hyde Park, New York, 11040, United States

RECRUITING

Weill Cornell Medical College - New York Presbyterian Hospital

New York, New York, 10065, United States

RECRUITING

American Thrombosis and Hemostasis Network

Rochester, New York, 14626, United States

RECRUITING

Montefiore Medical Center

The Bronx, New York, 10461, United States

RECRUITING

Comprehensive Hemophilia Treatment Center, University of North Carolina at Chapel Hill

Chapel Hill, North Carolina, 27517, United States

RECRUITING

St. Jude Affiliate Clinic at Novant Health Hemby Children's Hospital

Charlotte, North Carolina, 28204, United States

RECRUITING

East Carolina University Hemophilia Treatment Center

Greenville, North Carolina, 27834, United States

RECRUITING

Wake Forest University Health Sciences

Winston-Salem, North Carolina, 27157, United States

RECRUITING

Akron Children's Hospital - Showers Center for Cancer & Blood Disorders

Akron, Ohio, 44308, United States

RECRUITING

Cincinnati Children's Hospital Medical Center, Hemophilia & Thrombosis Center

Cincinnati, Ohio, 45229, United States

RECRUITING

University of Cincinnati Medical Center Hemophilia Treatment Center

Cincinnati, Ohio, 45267, United States

RECRUITING

University Hospitals Health System Cleveland

Cleveland, Ohio, 44106, United States

RECRUITING

Nationwide Children's Hospital Columbus

Columbus, Ohio, 43205, United States

RECRUITING

Dayton Children's Hemostasis and Thrombosis Center

Dayton, Ohio, 45404, United States

RECRUITING

Northwest Ohio Hemophilia Treatment Center at the Toledo Hospital

Toledo, Ohio, 43606, United States

RECRUITING

Children's Hospital of Philadelphia

Philadelphia, Pennsylvania, 19104, United States

RECRUITING

Penn Comprehensive Hemophilia and Thrombophilia Program/Hospital of the University of Pennsylvania

Philadelphia, Pennsylvania, 19104, United States

RECRUITING

Hemophilia Center of Western Pennsylvania

Pittsburgh, Pennsylvania, 15213, United States

RECRUITING

Rhode Island Hospital Hemostasis and Thrombosis Center

Providence, Rhode Island, 02903, United States

RECRUITING

St. Jude Children's Research Hospital

Memphis, Tennessee, 38105, United States

RECRUITING

Vanderbilt University Medical Center

Nashville, Tennessee, 37212, United States

RECRUITING

Children's Blood and Cancer Center of Central Texas

Austin, Texas, 78723, United States

RECRUITING

North Texas Hemophilia and Thrombosis Program - Pediatric Program / Center for Cancer & Blood Disorders

Dallas, Texas, 75235, United States

RECRUITING

North Texas Comprehensive Hemophilia Treatment Center

Dallas, Texas, 75390, United States

RECRUITING

Gulf States Hemophilia and Thrombophilia Center

Houston, Texas, 77030, United States

RECRUITING

Texas Children's Hemophilia & Thrombosis Center/Baylor College of Medicine

Houston, Texas, 77030, United States

RECRUITING

South Texas Comprehensive Hemophilia and Thrombophilia Treatment Center

San Antonio, Texas, 78229, United States

RECRUITING

Washington Center for Bleeding Disorders

Seattle, Washington, 98101, United States

RECRUITING

Hemophilia Outreach Center Green Bay

Green Bay, Wisconsin, 54311, United States

RECRUITING

Comprehensive Center for Bleeding Disorders

Milwaukee, Wisconsin, 53226, United States

RECRUITING

Related Publications (8)

  • Weijer C, Freedman B, Fuks A, Robbins J, Shapiro S, Skrutkowska M. What difference does it make to be treated in a clinical trial? A pilot study. Clin Invest Med. 1996 Jun;19(3):179-83.

    PMID: 8724821BACKGROUND
  • Braunholtz DA, Edwards SJ, Lilford RJ. Are randomized clinical trials good for us (in the short term)? Evidence for a "trial effect". J Clin Epidemiol. 2001 Mar;54(3):217-24. doi: 10.1016/s0895-4356(00)00305-x.

    PMID: 11223318BACKGROUND
  • West J, Wright J, Tuffnell D, Jankowicz D, West R. Do clinical trials improve quality of care? A comparison of clinical processes and outcomes in patients in a clinical trial and similar patients outside a trial where both groups are managed according to a strict protocol. Qual Saf Health Care. 2005 Jun;14(3):175-8. doi: 10.1136/qshc.2004.011478.

    PMID: 15933313BACKGROUND
  • Unger JM, Barlow WE, Martin DP, Ramsey SD, Leblanc M, Etzioni R, Hershman DL. Comparison of survival outcomes among cancer patients treated in and out of clinical trials. J Natl Cancer Inst. 2014 Mar;106(3):dju002. doi: 10.1093/jnci/dju002. Epub 2014 Mar 13.

    PMID: 24627276BACKGROUND
  • https://www.fda.gov/drugs/resources-information-approved-drugs/hematologyoncology-cancer-approvals-safety-notifications. Accessed 04 Jul 2019

    BACKGROUND
  • https://www.clinicaltrials.gov/ct2/results?cond=Hematologic+Diseases&term=&cntry=&state=&city=&dist=. Accessed 04 Jul 2019

    BACKGROUND
  • Konkle BA, Recht M; members of Working Group 2, the NHLBI State of the Science Workshop on factor VIII inhibitors: Generating a national blueprint for future research. The national blueprint for 21st century data and specimen collection and observational cohort studies: NHLBI State of the Science Workshop on factor VIII inhibitors. Haemophilia. 2019 Jul;25(4):590-594. doi: 10.1111/hae.13772.

    PMID: 31329362BACKGROUND
  • Iorio A, Keepanasseril A, Foster G, Navarro-Ruan T, McEneny-King A, Edginton AN, Thabane L; WAPPS-Hemo co-investigator network. Development of a Web-Accessible Population Pharmacokinetic Service-Hemophilia (WAPPS-Hemo): Study Protocol. JMIR Res Protoc. 2016 Dec 15;5(4):e239. doi: 10.2196/resprot.6558.

    PMID: 27977390BACKGROUND

Biospecimen

Retention: SAMPLES WITH DNA

All participants have the option to provide consent to have specimens stored in the ATHN Transcends Biorepository. Inhibitor titer testing will be performed locally (unless otherwise specified) as per standard of care which is generally expected to coincide with the following: * Baseline Visit * Annual Visit * Product switch * Suspected inhibitor development * Confirmatory test for previously elevated result * Study Exit * Additional timepoints per any modules Genetic testing (performed once) will be optional and provided by central labs, as funding allows, across all cohorts. Anti-drug antibodies testing - For participants receiving non-factor products (e.g., emicizumab) and if testing is clinically appropriate (suspicion of anti-drug antibodies forming), this specimen will be analyzed, as funding allows. Factor activity testing will be performed locally at the following timepoints: * Baseline visit * 6 and 18-month follow-up visits * Annual visit * Ad hoc * Study arm exit

MeSH Terms

Conditions

Hematologic DiseasesHemostatic DisordersConnective Tissue DiseasesHemophilia AThrombosisvon Willebrand DiseasesThrombophiliaBlood Platelet DisordersHemophilia BThalassemiaAnemia, Sickle Cell

Condition Hierarchy (Ancestors)

Hemic and Lymphatic DiseasesVascular DiseasesCardiovascular DiseasesHemorrhagic DisordersSkin and Connective Tissue DiseasesBlood Coagulation Disorders, InheritedBlood Coagulation DisordersCoagulation Protein DisordersGenetic Diseases, InbornCongenital, Hereditary, and Neonatal Diseases and AbnormalitiesEmbolism and ThrombosisGenetic Diseases, X-LinkedAnemia, Hemolytic, CongenitalAnemia, HemolyticAnemiaHemoglobinopathies

Study Officials

  • Michael Recht, MD, PhD, MBA

    Yale University School of Medicine & National Bleeding Disorders Foundation

    PRINCIPAL INVESTIGATOR
  • Tammuella Chrisentery-Singleton, MD

    ATHN, Ochsner Clinic Foundation

    PRINCIPAL INVESTIGATOR

Central Study Contacts

Carol Fedor, ND, RN, CCRC

CONTACT

Nana Ama Afari-Dwamena, MPH

CONTACT

Study Design

Study Type
observational
Observational Model
COHORT
Time Perspective
PROSPECTIVE
Sponsor Type
NETWORK
Responsible Party
SPONSOR

Study Record Dates

First Submitted

May 11, 2020

First Posted

May 21, 2020

Study Start

September 30, 2020

Primary Completion (Estimated)

June 1, 2035

Study Completion (Estimated)

December 1, 2035

Last Updated

January 12, 2026

Record last verified: 2026-01

Data Sharing

IPD Sharing
Will not share

Locations