NCT03853486

Brief Summary

ATHN 9 is a natural history study to assess the safety of various Von Willebrand Factor (VWF) regimens for different indications (on-demand, surgery and prophylaxis) in adult and pediatric participants with clinically severe congenital VWD.

Trial Health

75
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
108

participants targeted

Target at P50-P75 for all trials

Timeline
3mo left

Started Jun 2019

Longer than P75 for all trials

Geographic Reach
1 country

22 active sites

Status
active not recruiting

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Progress97%
Jun 2019Jul 2026

First Submitted

Initial submission to the registry

January 11, 2019

Completed
2 months until next milestone

First Posted

Study publicly available on registry

February 25, 2019

Completed
4 months until next milestone

Study Start

First participant enrolled

June 18, 2019

Completed
6.5 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

December 31, 2025

Completed
7 months until next milestone

Study Completion

Last participant's last visit for all outcomes

July 30, 2026

Expected
Last Updated

March 12, 2025

Status Verified

March 1, 2025

Enrollment Period

6.5 years

First QC Date

January 11, 2019

Last Update Submit

March 11, 2025

Conditions

Keywords

VWFvon Willebrand DiseaseVWDFactorATHN 9

Outcome Measures

Primary Outcomes (1)

  • Reported adverse events from VWF regimens for different indications (on-demand, surgery, and prophylaxis) as measured by EUHASS.

    Number of adverse events as measured by EUHASS as well as treatment-emergent side effects of therapy for various Von Willebrand Factor (VWF) regimens for different indications (on-demand, surgery and prophylaxis) in adult and pediatric participants with clinically severe congenital VWD.

    2 years

Secondary Outcomes (12)

  • Enrich and analyze data collected about AE events as defined by EUHASS using standardized diagnostic battery using an ELISA-based VWF assay.

    3 years

  • Enrich and analyze data collected about AE events, as defined by EUHASS using genetic sequence analysis of VWF coding regions and adjacent non-coding regions.

    2 years

  • Substudy modules will be developed to evaluate and report on cohorts of study participants who initiate treatment with specific product.

    2 years

  • Factor replacement used as prophylaxis.

    3 years

  • Capture bleeding events using the Pictorial Bleeding. Assessment Chart.

    3 years

  • +7 more secondary outcomes

Eligibility Criteria

Sexall
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)
Sampling MethodNon-Probability Sample
Study Population

This is a natural history study in which it is anticipated that approximately 130 participants will be enrolled. The study will attempt to enroll a target number of at least 30 participants who are receiving VONVENDI but will not mandate the use of VONVENDI.

You may qualify if:

  • Participants with severe Von Willebrand Disease with Type 3 VWD or VWF:RCo, VWF:GPlbM or VWF:Ag ≤30% of pooled normal control plasma on more than one occasion;
  • Participants with clinically severe VWD as defined by VWF:RCo, VWF:GPlbM or VWF:Ag ≤40% of normal with severe bleeding phenotype defined as requiring recurrent use of factor concentrates; and
  • Co-enrollment in the ATHNdataset.

You may not qualify if:

  • Diagnosis of platelet-type VWD;
  • Diagnosis of acquired VWD (clinical diagnosis based on association with hypothyroidism, lymphoproliferative and myeloproliferative disorders, malignancies and cardiovascular disease, typically aortic stenosis or LVAD).

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (22)

Center for Inherited Blood Disorders

Orange, California, 92868, United States

Location

University of Colorado Denver Hemophilia and Thrombosis Center

Aurora, Colorado, 80045, United States

Location

Connecticut Bleeding and Clotting Disorders Center

Farmington, Connecticut, 06030, United States

Location

University of Florida Hemophilia Treatment Center

Gainesville, Florida, 32610, United States

Location

Children's Healthcare of Atlanta/Emory

Atlanta, Georgia, 30322, United States

Location

Bleeding and Clotting Disorders Institute

Peoria, Illinois, 61615, United States

Location

Indiana Hemophilia and Thrombosis Center (IHTC)

Indianapolis, Indiana, 46260, United States

Location

Louisiana Center for Bleeding and Clotting Disorders

New Orleans, Louisiana, 70112, United States

Location

University of Michigan Hemophilia and Coagulation Disorders

Ann Arbor, Michigan, 48109, United States

Location

Children's Hospital of Michigan Hemostasis and Thrombosis Center

Detroit, Michigan, 48201, United States

Location

Michigan State University Center for Bleeding and Clotting Disorders

East Lansing, Michigan, 48823, United States

Location

Mayo Comprehensive Hemophilia Center

Rochester, Minnesota, 55905, United States

Location

Washington University Center for Treatment of Bleeding and Blood Clotting Disorders

St Louis, Missouri, 63110, United States

Location

Nationwide Children's Hospital Columbus

Columbus, Ohio, 43205, United States

Location

Oregon Health

Portland, Oregon, 91239, United States

Location

Pennsylvania Comprehensive Hemophilia and Thrombophilia Program / Hospital of the University of Pennsylvania

Philadelphia, Pennsylvania, 19104, United States

Location

Hemophilia Center of Western Pennsylvania

Pittsburgh, Pennsylvania, 15213, United States

Location

Rhode Island Hemostasis & Thrombosis Center

Providence, Rhode Island, 02903, United States

Location

University of Tennessee, University Clinical Health (Memphis)

Memphis, Tennessee, 38119, United States

Location

Vanderbilt University Medical Center

Nashville, Tennessee, 37212, United States

Location

Hemophilia Outreach Center

Green Bay, Wisconsin, 54311, United States

Location

Versiti - Blood Center of Wisconsin

Milwaukee, Wisconsin, 53201, United States

Location

Biospecimen

Retention: SAMPLES WITH DNA

All participants will undergo laboratory evaluation. The remaining specimen volume will be stored and may be used for future research. Specimens will be tested as follows: * FVIII Activity, VWF Antigen, and the VWF:GPIbM Activity Assay. Reflex testing may include: VWD Type 2B Binding, VWD Type 2N Binding, VWF Propeptide Antigen, and/or VWF Quantitative Multimers * Genetic sequence analysis of VWF coding regions and adjacent non-coding regions

MeSH Terms

Conditions

von Willebrand Diseases

Condition Hierarchy (Ancestors)

Blood Coagulation Disorders, InheritedBlood Coagulation DisordersHematologic DiseasesHemic and Lymphatic DiseasesCoagulation Protein DisordersBlood Platelet DisordersHemorrhagic DisordersGenetic Diseases, InbornCongenital, Hereditary, and Neonatal Diseases and Abnormalities

Study Officials

  • Robert Sidonio, MD

    Emory University / Children's Healthcare of Atlanta

    PRINCIPAL INVESTIGATOR
  • Angela Weyand, MD

    University of Michigan Hemophilia and Coagulation Disorders

    PRINCIPAL INVESTIGATOR

Study Design

Study Type
observational
Observational Model
COHORT
Time Perspective
PROSPECTIVE
Sponsor Type
NETWORK
Responsible Party
SPONSOR

Study Record Dates

First Submitted

January 11, 2019

First Posted

February 25, 2019

Study Start

June 18, 2019

Primary Completion

December 31, 2025

Study Completion (Estimated)

July 30, 2026

Last Updated

March 12, 2025

Record last verified: 2025-03

Data Sharing

IPD Sharing
Will not share

Locations