NCT02761915

Brief Summary

The purpose of this first in human study is to determine the safety and feasibility of 1RG-CART therapy in patients with relapsed or refractory neuroblastoma. 1RG-CART therapy is a novel immunotherapy under investigation in which patients have their T-cells (a type of white blood cell) collected and modified in the laboratory, before they are given back to the patient. The T-cells are modified to express a chimeric antigen receptor (CAR) which targets disialoganglioside (GD2), a marker expressed on the surface of neuroblastoma cells.

Trial Health

87
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
17

participants targeted

Target at below P25 for phase_1

Timeline
Completed

Started Feb 2016

Longer than P75 for phase_1

Geographic Reach
1 country

1 active site

Status
completed

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

First Submitted

Initial submission to the registry

February 24, 2016

Completed
5 days until next milestone

Study Start

First participant enrolled

February 29, 2016

Completed
2 months until next milestone

First Posted

Study publicly available on registry

May 4, 2016

Completed
4.6 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

December 16, 2020

Completed
Same day until next milestone

Study Completion

Last participant's last visit for all outcomes

December 16, 2020

Completed
8 months until next milestone

Results Posted

Study results publicly available

August 17, 2021

Completed
Last Updated

August 17, 2021

Status Verified

July 1, 2021

Enrollment Period

4.8 years

First QC Date

February 24, 2016

Results QC Date

June 15, 2021

Last Update Submit

July 23, 2021

Conditions

Keywords

NeuroblastomaImmunotherapy1RG-CARTCyclophosphamideFludarabineCAR T-cellsAnti-GD2GD2CARChimeric Antigen ReceptorCytokine Release Syndrome

Outcome Measures

Primary Outcomes (3)

  • To Evaluate the Feasibility of 1RG-CART Therapy in Patients With Relapsed or Refractory Neuroblastoma

    Feasibility of 1RG-CART therapy assessed as the number of patients who commence T-cell processing and are subsequently evaluable for 1RG-CART engraftment at Day 14.

    Day 14

  • Safety and Tolerability of 1RG-CART Therapy

    Number of serious adverse events, non-serious adverse events and adverse events that are related to fludarabine, cyclophosphamide or 1RG-CART.

    From the time of informed consent to leukapheresis until withdrawal from the trial or start of other anti-cancer therapy (a median time period of 132 days [range 68 to 301 days])

  • To Determine Recommended Phase II Regimen by Assessing the Number of DLTs at Each Dose Level

    Number of dose limiting toxicities (DLTs) at each dose level.

    From the time of informed consent to leukapheresis until withdrawal from the trial or start of other anti-cancer therapy (a median time period of 132 days [range 68 to 301 days])

Secondary Outcomes (6)

  • 1RG-CART Counts in the Peripheral Blood

    From Day 0 until end of trial (median 38.5 days, range 20 to 233 days)

  • Assessment of Tumour Response From Baseline (RECIST)

    Day 28, 2 months and 4 months

  • Assessment of Tumour Response From Baseline (irRC)

    Day 28, 2 months and 4 months

  • Assessment of Tumour Response From Baseline (INRC)

    Day 28, 2 months and 4 months

  • To Evaluate Anti-tumour Activity (Progression Free Survival)

    Up to 2 years

  • +1 more secondary outcomes

Study Arms (6)

Dose Level 1

OTHER

Patients in Dose Level 1 will receive 1x10\^7 1RG-CART/m\^2 intravenously (IV) on Day 0.

Other: LeukapheresisGenetic: 1RG-CART

Dose Level 2

OTHER

Patients in Dose Level 2 will receive 300 mg/m\^2/day of cyclophosphamide for four days (Days -4 to -1) followed by 1x10\^7 1RG-CART/m\^2 IV on Day 0.

Other: LeukapheresisDrug: CyclophosphamideGenetic: 1RG-CART

Dose Level 3

OTHER

Patients in Dose Level 3 will receive 300 mg/m\^2/day of cyclophosphamide for four days (Days -7 to -4) and 25 mg/m\^2/day of fludarabine for five days (Days -8 to -4), followed by 1x10\^7 1RG-CART/m\^2 IV on Day 0.

Other: LeukapheresisDrug: CyclophosphamideDrug: FludarabineGenetic: 1RG-CART

Dose Level 4

OTHER

Patients in Dose Level 4 will receive 300 mg/m\^2/day of cyclophosphamide for four days (Days -7 to -4) and 25 mg/m\^2/day of fludarabine for five days (Days -8 to -4), followed by 1x10\^8 1RG-CART/m\^2 IV on Day 0.

Other: LeukapheresisDrug: CyclophosphamideDrug: FludarabineGenetic: 1RG-CART

Dose Level 5

OTHER

If the required level of 1RG-CART survival is not reached, a further cohort of patients (Dose Level 5) will receive 300 mg/m\^2/day of cyclophosphamide for four days (Days -7 to -4) and 25 mg/m\^2/day of fludarabine for five days (Days -8 to -4), followed by 5-10x10\^8 1RG-CART/m\^2 IV which could be be split over two days (Day 0 and Day 1).

Other: LeukapheresisDrug: CyclophosphamideDrug: FludarabineGenetic: 1RG-CART

Patients who underwent leukapheresis but did not proceed to receive any IMP

OTHER

Patients who were enrolled and underwent leukapheresis but who did not receive any IMP.

Other: Leukapheresis

Interventions

Dose Level 1Dose Level 2Dose Level 3Dose Level 4Dose Level 5Patients who underwent leukapheresis but did not proceed to receive any IMP
Dose Level 2Dose Level 3Dose Level 4Dose Level 5
Dose Level 3Dose Level 4Dose Level 5
1RG-CARTGENETIC
Dose Level 1Dose Level 2Dose Level 3Dose Level 4Dose Level 5

Eligibility Criteria

Age1 Year+
Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)

You may qualify if:

  • Written informed consent\* for leukapheresis/venepuncture and transduction of T-cells.
  • Suitability for leukapheresis/venepuncture defined as:
  • Negative for human immunodeficiency virus (HIV), human T-cell lymphotropic virus (HTLV) 1, HTLV 2, syphilis and hepatitis B.
  • Minimum T-lymphocyte count of 0.25x10\^9/L.
  • Relapsed or refractory neuroblastoma (the patient must have evidence of active disease even if they do not currently require active treatment).
  • Patients must have at least one lesion that can be evaluated for response by imaging and/or diffuse bone marrow infiltration.
  • Adequate renal function, defined as a glomerular filtration rate (GFR) ≥ 30 mL/min/1.73m\^2 (corrected).
  • Karnofsky score ≥60% if ≥16 years old or Lansky performance score of ≥60% if \<16 years old
  • \*Informed consent from the patient's parent or legal guardian is required for all patients under 16 years of age. Patients under 16 years of age may also provide written assent to take part in the trial.

You may not qualify if:

  • Eligibility Criteria for the Main Trial
  • Histologically proven neuroblastoma, which is relapsed or refractory to conventional treatment.
  • Patients must have at least one lesion that can be evaluated for response by imaging and/or diffuse bone marrow infiltration.
  • Aged ≥12 months at the time written consent is given for the dose escalation phase or aged ≥6 months at the time written consent is given for the dose expansion phase of the trial.
  • Life expectancy of at least two months.
  • Karnofsky score ≥60% if ≥16 years old or Lansky performance score of ≥60% if \<16 years old
  • Adequate renal function, defined as a GFR of ≥30 mL/min/1.73m\^2 (corrected).
  • Written (signed and dated) informed consent to the main trial\* and be capable of co-operating with treatment and follow-up.
  • \*Informed consent from the patient's parent or legal guardian is required for all patients under 16 years of age. Patients under 16 years of age may also provide written assent to take part in the trial.
  • Patients who have received anti-GD2 antibody treatment within the previous 2 weeks (based on the half life of ch14.18 antibody being 1-3 days in children); patients who have received dinutuximab or other anti-GD2-directed antibody may need a longer washout period.
  • Patients for whom rituximab is contraindicated due to severe previous hypersensitivity or any other reason.
  • Patients must have recovered from the acute reversible effects of any previous therapy before infusion of the 1RG-CART.
  • Current CNS involvement (including intradural meningeal involvement). Patients who previously had CNS involvement but have been surgically treated and disease free for ≥2 months are eligible.
  • Co-existing chronic progressive neurological disease.
  • Airway compromise by direct tumoural invasion or compression.
  • +9 more criteria

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (1)

University College London Institute of Child Health & Great Ormond Street Hospital

London, WC1N 3JH, United Kingdom

Location

Related Publications (2)

  • Straathof K, Flutter B, Wallace R, Jain N, Loka T, Depani S, Wright G, Thomas S, Cheung GW, Gileadi T, Stafford S, Kokalaki E, Barton J, Marriott C, Rampling D, Ogunbiyi O, Akarca AU, Marafioti T, Inglott S, Gilmour K, Al-Hajj M, Day W, McHugh K, Biassoni L, Sizer N, Barton C, Edwards D, Dragoni I, Silvester J, Dyer K, Traub S, Elson L, Brook S, Westwood N, Robson L, Bedi A, Howe K, Barry A, Duncan C, Barone G, Pule M, Anderson J. Antitumor activity without on-target off-tumor toxicity of GD2-chimeric antigen receptor T cells in patients with neuroblastoma. Sci Transl Med. 2020 Nov 25;12(571):eabd6169. doi: 10.1126/scitranslmed.abd6169.

    PMID: 33239386BACKGROUND
  • Li X, Li W, Xu L, Song Y. Chimeric antigen receptor-immune cells against solid tumors: Structures, mechanisms, recent advances, and future developments. Chin Med J (Engl). 2024 Jun 5;137(11):1285-1302. doi: 10.1097/CM9.0000000000002818. Epub 2023 Aug 28.

MeSH Terms

Conditions

RecurrenceNeuroblastomaCytokine Release Syndrome

Interventions

LeukapheresisCyclophosphamidefludarabine

Condition Hierarchy (Ancestors)

Disease AttributesPathologic ProcessesPathological Conditions, Signs and SymptomsNeuroectodermal Tumors, Primitive, PeripheralNeuroectodermal Tumors, PrimitiveNeoplasms, NeuroepithelialNeuroectodermal TumorsNeoplasms, Germ Cell and EmbryonalNeoplasms by Histologic TypeNeoplasmsNeoplasms, Glandular and EpithelialNeoplasms, Nerve TissueSystemic Inflammatory Response SyndromeInflammationShock

Intervention Hierarchy (Ancestors)

CytapheresisBiological TherapyTherapeuticsBlood Component RemovalLeukocyte Reduction ProceduresCell SeparationCytological TechniquesClinical Laboratory TechniquesInvestigative TechniquesPhosphoramide MustardsNitrogen Mustard CompoundsMustard CompoundsHydrocarbons, HalogenatedHydrocarbonsOrganic ChemicalsPhosphoramidesOrganophosphorus Compounds

Limitations and Caveats

For the secondary outcome measure of Overall Survival, one patient from Dose Level 1 withdrew consent to continue with the trial, therefore the time to death (if applicable) for this patient was not collected.

Results Point of Contact

Title
Regulatory Affairs Manager
Organization
Cancer Research UK Centre for Drug Development

Study Officials

  • John Anderson, Prof

    University College London Institute of Child Health & Great Ormond Street Hospital

    PRINCIPAL INVESTIGATOR

Publication Agreements

PI is Sponsor Employee
No
Restrictive Agreement
No

Study Design

Study Type
interventional
Phase
phase 1
Allocation
NON RANDOMIZED
Masking
NONE
Purpose
TREATMENT
Intervention Model
SEQUENTIAL
Sponsor Type
OTHER
Responsible Party
SPONSOR

Study Record Dates

First Submitted

February 24, 2016

First Posted

May 4, 2016

Study Start

February 29, 2016

Primary Completion

December 16, 2020

Study Completion

December 16, 2020

Last Updated

August 17, 2021

Results First Posted

August 17, 2021

Record last verified: 2021-07

Data Sharing

IPD Sharing
Will not share

Locations