NCT07040774

Brief Summary

Type I interferonopathies are rare autoinflammatory disorders caused by genetic defects and associated with significant morbidity and mortality. These diseases are refractory to conventional immunosuppressive therapies. They typically occur in childhood, although disease onset in adulthood has been observed. The clinical spectrum is wide and mainly involves the central nervous system. Joint involvement is also common, and more rarely, haematological features such as cytopenias or immunodeficiency may be observed. Nearly all patients show consistent over-activation of the type I IFN pathway, as evidenced, the expression of IFN-stimulated genes, the so-called 'interferon signature'. To date, the natural history of interferonopathies remains unclear. In this context, the establishment of a natural history of type I interferonopathy in patients is proposed to elucidate the pathophysiological mechanisms and identify biomarkers for diagnosis, prognosis, and disease activity, with the aim of better characterising the diversity of interferonopathies. The main objective is to characterise the evolution of the pathology in paediatric and adult patients with type I interferonopathies. The overall aim of this research is to propose therapeutic options tailored to patient phenotypes and to better define patient sub-groups in order to optimise the preparation of future clinical trials.

Trial Health

88
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
500

participants targeted

Target at P75+ for all trials

Timeline
235mo left

Started Oct 2025

Longer than P75 for all trials

Geographic Reach
11 countries

32 active sites

Status
recruiting

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Progress4%
Oct 2025Oct 2045

First Submitted

Initial submission to the registry

June 12, 2025

Completed
15 days until next milestone

First Posted

Study publicly available on registry

June 27, 2025

Completed
3 months until next milestone

Study Start

First participant enrolled

October 1, 2025

Completed
20 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

October 1, 2045

Expected
Same day until next milestone

Study Completion

Last participant's last visit for all outcomes

October 1, 2045

Last Updated

May 13, 2026

Status Verified

May 1, 2026

Enrollment Period

20 years

First QC Date

June 12, 2025

Last Update Submit

May 12, 2026

Conditions

Keywords

Immune dysfuntionNeurological diseaseAutoimmune diseasesGenetics diseasesInterferonAicardi-Goutieres Syndrom

Outcome Measures

Primary Outcomes (1)

  • Characterizing disease progression in pediatric and adult patients with type I interferonopathies

    Composite description of phenotypes of patients with type I interferonopathies according to genotype (clinical, biological) over time.

    2025-2045

Secondary Outcomes (3)

  • Identifing and characterising genotype-specific immunological factors

    2025-2045

  • Research of biomarkers for diagnosis, prognosis and monitoring of disease activity

    2025-2045

  • Monitoring of treatment response according to phenotype and genotype

    2025-2045

Study Arms (1)

Patients

Patients with genetically confirmed type I interferonopathy

Eligibility Criteria

Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)
Sampling MethodNon-Probability Sample
Study Population

Patients with genetically confirmed type I interferonopathy in Europe. 500 patients estimated.

You may qualify if:

  • Genetically confirmed patient with type I interferonopathy
  • Patient affiliated to a social security scheme or beneficiary of such a scheme.

You may not qualify if:

  • \- Opposition of the patient and/or parental authority if the patient is a minor, to participation in the study.

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (32)

Medical University Innsbruck

Innsbruck, Austria

NOT YET RECRUITING

Antwerp University Hospital

Antwerp, Belgium

NOT YET RECRUITING

Children's Hospital Zagreb

Zagreb, Croatia

NOT YET RECRUITING

Motol University Hospital

Prague, Czechia

NOT YET RECRUITING

CHU d'Angers

Angers, 49000, France

RECRUITING

Hôpital de Mercy - CHR Metz Thionville

Ars-Laquenexy, 57530, France

RECRUITING

CHU de Besançon

Besançon, 25030, France

RECRUITING

CHU de Bordeaux

Bordeaux, France

NOT YET RECRUITING

CHU Morvan

Brest, 29200, France

RECRUITING

Hôpital Femme Mère Enfant - HCL

Bron, 69500, France

RECRUITING

CHU de Dijon

Dijon, 21231, France

NOT YET RECRUITING

Hôpitaux Nord Ouest Villefranche

Gleizé, 69400, France

RECRUITING

Hôpital Bicêtre

Le Kremlin-Bicêtre, 94270, France

NOT YET RECRUITING

Hôpital Claude Huriez, CHU de Lille

Lille, 59000, France

NOT YET RECRUITING

APHM Hôpitaux de Marseille

Marseille, France

RECRUITING

CHU de Montpellier

Montpellier, 34295, France

RECRUITING

CHRU Nancy

Nancy, France

RECRUITING

CHU de Nantes

Nantes, 44000, France

RECRUITING

CH Agen-Nérac

Nérac, 47600, France

RECRUITING

Hôpital de l'Archet

Nice, 06200, France

RECRUITING

Hôpital Armand Trousseau

Paris, 75012, France

NOT YET RECRUITING

Hôpital Bichat

Paris, 75018, France

NOT YET RECRUITING

Hôpital Robert Debré

Paris, 75019, France

NOT YET RECRUITING

Hôpital des Enfants - CHU de Toulouse

Toulouse, 31300, France

RECRUITING

Hôpital Necker Enfants Malades

Paris, Île-de-France Region, 75015, France

RECRUITING

University of Tübingen

Tübingen, Germany

NOT YET RECRUITING

Meyer Children's Hospital IRCCS

Florence, Italy

NOT YET RECRUITING

Hospital Universitari Vall d'Hebron

Barcelona, Spain

NOT YET RECRUITING

Hospital Universitario Son Espases

Palma de Mallorca, Spain

NOT YET RECRUITING

Karolinska University Hospital

Stockholm, Sweden

NOT YET RECRUITING

Hacettepe İhsan Doğramacı Children's Hospital

Ankara, Turkey (Türkiye)

RECRUITING

Leeds Teaching Hospitals NHS Trust

Leeds, United Kingdom

NOT YET RECRUITING

MeSH Terms

Conditions

Genetic Diseases, InbornImmune System DiseasesAutoimmune DiseasesNervous System Diseases

Condition Hierarchy (Ancestors)

Congenital, Hereditary, and Neonatal Diseases and Abnormalities

Central Study Contacts

Study Design

Study Type
observational
Observational Model
COHORT
Time Perspective
CROSS SECTIONAL
Sponsor Type
OTHER
Responsible Party
SPONSOR

Study Record Dates

First Submitted

June 12, 2025

First Posted

June 27, 2025

Study Start

October 1, 2025

Primary Completion (Estimated)

October 1, 2045

Study Completion (Estimated)

October 1, 2045

Last Updated

May 13, 2026

Record last verified: 2026-05

Locations