NCT06431893

Brief Summary

The goal of this long-term extension (LTE) study is to evaluate the safety and efficacy of pegtibatinase in patients with classical homocystinuria (HCU). Patients who are active in the Phase 1/2 COMPOSE study or those who complete the 24 weeks of blinded treatment in the Phase 3 HARMONY are eligible to participate. Participants will be in this clinical study for a minimum of 108 weeks including:

  • a treatment period of up to 104 weeks
  • a 4-week safety follow-up period

Trial Health

87
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
100

participants targeted

Target at P25-P50 for phase_3

Timeline
49mo left

Started Apr 2024

Longer than P75 for phase_3

Geographic Reach
14 countries

52 active sites

Status
enrolling by invitation

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Progress36%
Apr 2024Aug 2030

Study Start

First participant enrolled

April 30, 2024

Completed
8 days until next milestone

First Submitted

Initial submission to the registry

May 8, 2024

Completed
21 days until next milestone

First Posted

Study publicly available on registry

May 29, 2024

Completed
6.2 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

August 1, 2030

Expected
Same day until next milestone

Study Completion

Last participant's last visit for all outcomes

August 1, 2030

Last Updated

May 28, 2026

Status Verified

May 1, 2026

Enrollment Period

6.3 years

First QC Date

May 8, 2024

Last Update Submit

May 27, 2026

Conditions

Keywords

Classical homocystinuriaHCUCystathionine Beta Synthase Deficiency

Outcome Measures

Primary Outcomes (4)

  • Treatment-emergent AEs

    Incidence of treatment-emergent AEs

    Week 1 - Week 108

  • Hypermethioninemia

    Incidence of hypermethioninemia

    Week 1 - Week 108

  • Hypomethioninemia

    Incidence of hypomethioninemia

    Week 1 - Week 108

  • Dietary Protein Rescue

    Proportion of participants requiring dietary protein rescue for participants with hypomethioninemia

    Week 1 - Week 108

Secondary Outcomes (3)

  • Maximum Drug Concentration

    Pharmacokinetic Assessment Period - 4 weeks & 8 weeks

  • Area under the Curve within the Dosing Interval

    Pharmacokinetic Assessment Period - 4 weeks & 8 weeks

  • Total Homocysteine (tHcy) Levels

    Week 1 - Week 108

Study Arms (1)

pegtibatinase

EXPERIMENTAL
Drug: Pegtibatinase

Interventions

Pegtibatinase BIW

Also known as: OT-58, TVT-058
pegtibatinase

Eligibility Criteria

Age5 Years - 65 Years
Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)

You may qualify if:

  • Participants active in the COMPOSE study or who completed the 24-week blinded period on study intervention (pegtibatinase or placebo) in the Phase 3 HARMONY study

You may not qualify if:

  • Participant permanently discontinued from study intervention treatment in a previous pegtibatinase study due to serious AE (SAE) or intolerance

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (52)

Phoenix Children's Hospital

Phoenix, Arizona, 85006, United States

Location

Yale University School of Medicine

New Haven, Connecticut, 06519, United States

Location

Emory University

Atlanta, Georgia, 30322, United States

Location

Ann & Robert H. Lurie Children's Hospital of Chicago

Chicago, Illinois, 60611, United States

Location

Maine Health Pediatric Specialty Care

Portland, Maine, 04012, United States

Location

Uncommon Cures

Chevy Chase, Maryland, 20815, United States

Location

Icahn School of Medicine at Mount Sinai

New York, New York, 10029, United States

Location

Science 37 - Virtual Site

Morrisville, North Carolina, 27560, United States

Location

Oregon Health and Science University

Portland, Oregon, 97239, United States

Location

The Children's Hospital of Philadelphia

Philadelphia, Pennsylvania, 19104, United States

Location

University of Pittsburgh Medical Center - Children's Hospital of Pittsburgh

Pittsburgh, Pennsylvania, 15224, United States

Location

University of Texas Southwestern Medical Center

Dallas, Texas, 75390, United States

Location

Utah Health - The University of Utah Primary Children's Hospital

Salt Lake City, Utah, 84113, United States

Location

Royal Adelaide Hospital

Adelaide, Australia

Location

Royal Children's Hospital Melbourne

Parkville, Australia

Location

Westmead Hospital

Westmead, Australia

Location

Cliniques Universitaires Saint-Luc

Brussels, Belgium

Location

Universitair Ziekenhuis Antwerpen (UZA)

Edegem, Belgium

Location

Assistance Publique - Hôpitaux de Paris (AP-HP) - Hôpital Necker-Enfants Malades

Paris, France

Location

CHRU Hôpitaux de Tours - Hôpital Bretonneau

Tours, France

Location

Centre Hospitalier Régional Universitaire de Nancy (CHRU) - Hopitaux de Brabois - Hôpital d'enfants

Vandœuvre-lès-Nancy, France

Location

Universitätsklinikum Hamburg-Eppendorf

Hamburg, Germany

Location

Universitätsklinikum Leipzig

Leipzig, Germany

Location

Universitätsklinikum Münster

Münster, Germany

Location

Children's Health Ireland (CHI) at Temple Street

Dublin, Ireland

Location

Ospedale Pediatrico Giovanni XXIII

Bari, Italy

Location

IRCCS Istituto Giannina Gaslini

Genova, Italy

Location

Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico (Policlinico di Milano)

Milan, Italy

Location

Fondazione IRCCS San Gerardo Dei Tintori - Ospedale San Gerardo

Monza, Italy

Location

Azienda Ospedaliera di Padova

Padova, Italy

Location

SP ZOZ Szpital Uniwersytecki w Krakowie

Krakow, Poland

Location

Instytut Matki i Dziecka

Warsaw, Poland

Location

Instytut Pomnik-Centrum Zdrowia Dziecka

Warsaw, Poland

Location

Unidade Local de Saúde de Coimbra, EPE - Hospitais da Universidade de Coimbra

Coimbra, Portugal

Location

Unidade Local de Saúde de Santa Maria, EPE - Hospital de Santa Maria

Lisbon, Portugal

Location

Unidade Local de Saúde de São João, EPE - Hospital São João

Porto, Portugal

Location

Hamad General Hospital

Doha, Qatar

Location

Sidra Hospital

Doha, Qatar

Location

King Abdullah International Medical Research Center

Riyadh, Saudi Arabia

Location

King Faisal Specialist Hospital and Research Centre (KFSHRC) - Riyadh

Riyadh, Saudi Arabia

Location

Hospital Sant Joan de Déu

Barcelona, Spain

Location

Hospital Universitario 12 de Octubre

Madrid, Spain

Location

Hospital Universitario Ramón y Cajal

Madrid, Spain

Location

Complejo Hospitalario Universitario de Santiago (CHUS) - Hospital Clínico Universitario

Santiago de Compostela, Spain

Location

Hospital Universitario Virgen del Rocío

Seville, Spain

Location

Gazi University Hospital

Ankara, Turkey (Türkiye)

Location

Ege Üniversitesi Hastanesi Bornova

Bornova, Turkey (Türkiye)

Location

Istanbul University Cerrahpasa Hospital

Istanbul, Turkey (Türkiye)

Location

Birmingham Women's and Children's NHS Foundation Trust

Birmingham, United Kingdom

Location

University Hospitals Birmingham NHS Foundation Trust - Queen Elizabeth Hospital Birmingham

Birmingham, United Kingdom

Location

University College London Hospitals NHS Foundation Trust - National Hospital for Neurology and Neurosurgery

London, United Kingdom

Location

Salford Royal NHS Foundation Trust - Salford Royal Hospital

Salford, United Kingdom

Location

MeSH Terms

Conditions

Homocystinuria

Condition Hierarchy (Ancestors)

Brain Diseases, Metabolic, InbornBrain Diseases, MetabolicBrain DiseasesCentral Nervous System DiseasesNervous System DiseasesHyperhomocysteinemiaAmino Acid Metabolism, Inborn ErrorsMetabolism, Inborn ErrorsGenetic Diseases, InbornCongenital, Hereditary, and Neonatal Diseases and AbnormalitiesConnective Tissue DiseasesSkin and Connective Tissue DiseasesMetabolic DiseasesNutritional and Metabolic Diseases

Study Officials

  • Michael Imperiale, MD

    Travere Therapeutics, Inc.

    STUDY DIRECTOR

Study Design

Study Type
interventional
Phase
phase 3
Allocation
NA
Masking
NONE
Purpose
TREATMENT
Intervention Model
SINGLE GROUP
Sponsor Type
INDUSTRY
Responsible Party
SPONSOR

Study Record Dates

First Submitted

May 8, 2024

First Posted

May 29, 2024

Study Start

April 30, 2024

Primary Completion (Estimated)

August 1, 2030

Study Completion (Estimated)

August 1, 2030

Last Updated

May 28, 2026

Record last verified: 2026-05

Data Sharing

IPD Sharing
Will share

Requests for clinical trial data, including language stating its intended use, should be directed to datarequest@travere.com. If approved, the requested information will be provided to the requestor after signing a data access agreement. Requests can be made following completion of the study and full publication of the study data in a peer reviewed journal for up to 36 months following its publication. Travere reserves the right to decline or recommend modifications to a request if it does not comply with the data sharing policy or if it is determined that the request is made by a biased source.

Time Frame
Requests can be made following completion of the study and full publication of the study data in a peer reviewed journal for up to 36 months following its publication.
Access Criteria
Requires submission and approval of intended use and a data sharing agreement.

Locations