NCT06351462

Brief Summary

The long term burden of morbidity and mortality in the natural history of sickle cell disease has not been compared up to date to the risks and mortality of a curative option like bone marrow transplantation in severe sickle-cell disease patients. Given this lack of data, primary-care Sickle Cell Disease (SCD) physicians and transplant physicians are prevented from a factual debate over the benefit/risk ratio for each patient and refining indications of transplant in patients. Therefore, the present study seeks to describe and compare the very long-term outcomes after either Human Leukocyte Antigen (HLA) -matched sibling transplantation (study arm) and "non-transplant care" for severe sickle cell disease SCA patients in order to yield robust comparative data regarding both arms. The main objective is to assess the benefit of Hematopoietic stem cell transplantation (HSCT) regarding quality of life compared to standard care after 10 years, in patients with severe Sickle Cell Disease (SCD).

Trial Health

65
Monitor

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
220

participants targeted

Target at P75+ for not_applicable

Timeline
12mo left

Started May 2024

Typical duration for not_applicable

Status
not yet recruiting

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

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Study Timeline

Key milestones and dates

Study Progress67%
May 2024May 2027

First Submitted

Initial submission to the registry

April 2, 2024

Completed
6 days until next milestone

First Posted

Study publicly available on registry

April 8, 2024

Completed
23 days until next milestone

Study Start

First participant enrolled

May 1, 2024

Completed
3 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

May 1, 2027

Expected
Same day until next milestone

Study Completion

Last participant's last visit for all outcomes

May 1, 2027

Last Updated

April 19, 2024

Status Verified

December 1, 2023

Enrollment Period

3 years

First QC Date

April 2, 2024

Last Update Submit

April 17, 2024

Conditions

Keywords

Hematopoietic stem cell transplantation

Outcome Measures

Primary Outcomes (1)

  • Evaluation of quality of life assessed by SF36

    It will be assessed by the Short-form 36 (SF36) scale. The Short Form (36) Health Survey is a 36-item measure if health status. The score obtained varies between 0 and 100. The higher the score the less disability. Ware JE, Sherbourne CD. The Medical Outcomes Study 36-item short-form health survey (SF-36): I. Conceptual framework and item selection. Med Care 1992;30:473-83.

    10 years after HSCT

Secondary Outcomes (3)

  • Evaluation of gonadal function

    10 years after HSCT

  • Evaluation of quality of life

    10 years after HSCT

  • Proportion of patients with anxiety and depression

    10 years after HSCT

Study Arms (2)

Patients transplanted from allogeneic HLA-compatible sibling donor or from sibling cord blood unit

OTHER
Other: SpermogramOther: Hospital Anxiety and Depression Scale (HADS)Other: SF36 Quality of life questionnaireOther: Psychologist interviewOther: Optional sera bankingOther: Optional DNA banking

Controlled patients - not transplanted

OTHER
Other: SpermogramOther: Hospital Anxiety and Depression Scale (HADS)Other: SF36 Quality of life questionnaireOther: Psychologist interviewOther: Optional sera bankingOther: Optional DNA banking

Interventions

Spermogram will be proposed to men

Controlled patients - not transplantedPatients transplanted from allogeneic HLA-compatible sibling donor or from sibling cord blood unit

Anxiety and depression will be evaluated 10 years after HSCT

Controlled patients - not transplantedPatients transplanted from allogeneic HLA-compatible sibling donor or from sibling cord blood unit

Quality of life will be evaluated 10 years after HSCT

Controlled patients - not transplantedPatients transplanted from allogeneic HLA-compatible sibling donor or from sibling cord blood unit

During a follow-up visit

Controlled patients - not transplantedPatients transplanted from allogeneic HLA-compatible sibling donor or from sibling cord blood unit

One in the study

Controlled patients - not transplantedPatients transplanted from allogeneic HLA-compatible sibling donor or from sibling cord blood unit

Once in the study

Controlled patients - not transplantedPatients transplanted from allogeneic HLA-compatible sibling donor or from sibling cord blood unit

Eligibility Criteria

Age15 Years - 80 Years
Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)

You may qualify if:

  • Study population (exposed-patients), all criteria should be fulfilled:
  • Patients alive with Sickle Cell Anemia (SCA, meaning SS and Sbeta0 sickle cell anemia genotype)
  • Patients transplanted from allogeneic HLA-compatible sibling donor or from sibling cord blood unit from the 1st of January 2000 and the 31st of December 2012, whatever the age at transplant
  • Patients having received conditioning regimen containing busulfan 1mg/kg/dose (or equivalent adjusted body-weight dosage according to recommendation) x 16 doses + cyclophosphamide 200mg/kg total dose + anti-thymoglobuline
  • For patient under 18 years at time of enrolment, signed informed consent from both parental representatives
  • For patient aged 18 years old : signed informed consent
  • Having an affiliation to a social security regime
  • Control-population (Non-exposed patients) :
  • For each allografted patient, one non-exposed patient will be matched, based on the following criteria:
  • Gender
  • Age at the date of transplantation of the exposed patient (+/- 1 year)
  • Foetal hemoglobin (HbF) level (+/- 3%) before treatment intensification (defined as the initiation of either hydroxyurea or a transfusion program)
  • Hb level (+/- 0,9 g/dl) before treatment intensification
  • For patient under 18 years at time of enrolment, signed informed consent from both parental representatives
  • For patient above 18 years of age: signed informed consent
  • +1 more criteria

You may not qualify if:

  • Study population:
  • Transplantation from donor other than sibling or related cord-blood
  • Conditioning regimen other than busulfan 16mg/kg total dose + cyclophosphamide 200mg/kg total dose + anti-thymoglobuline
  • For both population:
  • Absence of signed informed consent
  • Having any debilitating medical or psychiatric illness, which preclude understanding of the inform consent as well as optimal treatment and follow-up

Contact the study team to confirm eligibility.

Sponsors & Collaborators

MeSH Terms

Conditions

Anemia, Sickle Cell

Interventions

4-amino-4'-hydroxylaminodiphenylsulfone

Condition Hierarchy (Ancestors)

Anemia, Hemolytic, CongenitalAnemia, HemolyticAnemiaHematologic DiseasesHemic and Lymphatic DiseasesHemoglobinopathiesGenetic Diseases, InbornCongenital, Hereditary, and Neonatal Diseases and Abnormalities

Central Study Contacts

Jean-Hugues Dalle, Pr

CONTACT

Jérôme Lambert, Pr

CONTACT

Study Design

Study Type
interventional
Phase
not applicable
Allocation
NON RANDOMIZED
Masking
NONE
Purpose
OTHER
Intervention Model
PARALLEL
Sponsor Type
OTHER
Responsible Party
SPONSOR

Study Record Dates

First Submitted

April 2, 2024

First Posted

April 8, 2024

Study Start

May 1, 2024

Primary Completion (Estimated)

May 1, 2027

Study Completion (Estimated)

May 1, 2027

Last Updated

April 19, 2024

Record last verified: 2023-12