NCT06806813

Brief Summary

The RICMAF Study is an observational, multicenter, non-pharmacological study conducted in Italy. Although Anderson-Fabry Disease (AFD) is rare, it is likely underdiagnosed due to its nonspecific symptoms, leading to delays in proper treatment. The RICMAF Study aims to improve understanding of AFD, especially its cardiac manifestations, which are a major cause of mortality. By gathering data from a large, nationwide patient registry, this study seeks to answer key questions about AFD's clinical course and improve patient outcomes. The primary goals of the RICMAF Study are:

  • To analyze the clinical profile, prevalence, and incidence of AFD, along with patients' family history and disease progression.
  • To identify early markers of cardiac involvement and predictors of cardiovascular complications to personalize care.
  • To investigate the relationship between genetic mutations, clinical presentation, and prognosis.
  • To find early indicators of organ damage through laboratory and imaging tests. All patients diagnosed with AFD following international guidelines are eligible.

Trial Health

77
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
800

participants targeted

Target at P75+ for all trials

Timeline
66mo left

Started Jan 2022

Longer than P75 for all trials

Geographic Reach
1 country

54 active sites

Status
recruiting

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Progress46%
Jan 2022Dec 2031

Study Start

First participant enrolled

January 26, 2022

Completed
3 years until next milestone

First Submitted

Initial submission to the registry

January 9, 2025

Completed
26 days until next milestone

First Posted

Study publicly available on registry

February 4, 2025

Completed
6 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

January 31, 2031

Expected
11 months until next milestone

Study Completion

Last participant's last visit for all outcomes

December 31, 2031

Last Updated

February 4, 2025

Status Verified

November 1, 2024

Enrollment Period

9 years

First QC Date

January 9, 2025

Last Update Submit

January 28, 2025

Conditions

Keywords

Fabry

Outcome Measures

Primary Outcomes (1)

  • Definition of Fabry disease natural history

    * Prevalence of Fabry disease: number of diagnosed cases of Fabry disease per 100,000 individuals in the general population. * Incidence of Fabry disease: number of new cases of Fabry disease per year per 100,000 individuals in the general population. * Number of patients with morbidity (heart failure, arrhythmias, kidney failure, stroke) and mortality (cardiac and non cardiac death) events recorded during follow-up.

    From enrollment to mean follow-up of 5 years.

Secondary Outcomes (3)

  • Fabry disease cardiac risk stratification

    From enrollment to mean follow-up of 5 years.

  • Correlation between genotype and cardiac involvement (ECG changes, LVH, T1/T2 mapping)/cardiac events.

    From enrollment to mean follow-up of 5 years.

  • Identification of biomarkers for early diagnosis in Fabry disease

    From enrollment to mean follow-up of 5 years.

Eligibility Criteria

Age2 Years+
Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)
Sampling MethodNon-Probability Sample
Study Population

All patients affected by AFD, diagnosed according to current international guidelines, will be included in the study, after obtaining free and informed consent. The study plans, based on the estimated prevalence of the disease, to enroll approximately 800 patients over the course of 10 years.

You may qualify if:

  • Patients diagnosed with Anderson Fabry disease
  • Age ≥ 2 years at diagnosis
  • Obtaining informed consent from the patient and parent or legal guardian.

You may not qualify if:

  • \- None

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (54)

ASL 2 Chieti - Ospedale Policlinico SS. Annunziata

Chieti, Abruzzo/Chieti, 66100, Italy

NOT YET RECRUITING

Azienda Ospedaliera Regionale S.Carlo

Potenza, Basilicata/Potenza, 85100, Italy

NOT YET RECRUITING

AORN "Sant'Anna e San Sebastiano" di Caserta

Caserta, Caserta, 81100, Italy

NOT YET RECRUITING

Azienda Ospedaliero - Universitaria "Mater Domini

Catanzaro, Catanzaro, 88100, Italy

NOT YET RECRUITING

Azienda Ospedaliera di Cosenza Università della Calabria

Cosenza, Cosenza, 87100, Italy

NOT YET RECRUITING

IRCCS Azienda Ospedaliero-Universitaria di Bologna

Bologna, EmiliaRomagna/Bologna, 40138, Italy

RECRUITING

IRCCS Ospedale Policlinico San Martino

Genova, Genova, Italy

NOT YET RECRUITING

ASST Papa Giovanni XXIII

Bergamo, Lombardia/Bergamo, 24127, Italy

RECRUITING

U.O.Cardiologia Spetali Civili 1

Brescia, Lombardia/Brescia, 25123, Italy

NOT YET RECRUITING

IRCCS Ospedale Maggiore Policlinico di Milano

Milan, Lombardia/Milano, 20122, Italy

NOT YET RECRUITING

IRCCS San Gerardo dei Tintori - S.C. Nefrologia, Monza - Università di Milano Bicocca

Milan, Lombardia/Milano, 20126, Italy

NOT YET RECRUITING

Centro Cardiologico Monzino

Milan, Lombardia/Milano, 20138, Italy

RECRUITING

Ospedale Niguarda

Milan, Lombardia/Milano, 20162, Italy

NOT YET RECRUITING

IRCCS Policlinico San Donato

San Donato Milanese, Lombardia/Milano, 20097, Italy

NOT YET RECRUITING

A O Universitaria Ospedali Riuniti Ancona

Ancona, Marche/Ancona, 60126, Italy

RECRUITING

Clinica cardiologica AZ ospedaliera Torrette

Ancona, Marche/Ancona, 60126, Italy

NOT YET RECRUITING

AO Dei Colli - Ospedale Monaldi

Napoli, Napoli, 80131, Italy

RECRUITING

AOU Policlinico

Napoli, Napoli, 80131, Italy

NOT YET RECRUITING

Azienda Ospedaliero-Universitaria di Parma

Parma, Parma, 43126, Italy

NOT YET RECRUITING

Azienda Ospedaliera "Guglielmo da Saliceto" di Piacenza

Piacenza, Piacenza, 29121, Italy

NOT YET RECRUITING

Ospedale Ivrea

Ivrea, Piemonte/Ivrea, 10015, Italy

NOT YET RECRUITING

Ospedale Maggiore della Carità

Novara, Piemonte/Novara, 28100, Italy

NOT YET RECRUITING

Molinette

Torino, Piemonte/Torino, 10134, Italy

RECRUITING

Ospedale Koelliker di Torino

Torino, Piemonte/Torino, 10134, Italy

NOT YET RECRUITING

Policlinico Bari

Bari, Puglia/Bari, 70124, Italy

RECRUITING

A O Universitaria Ospedali Riuniti di Foggia

Foggia, Puglia/Foggia, 71122, Italy

NOT YET RECRUITING

Ospedale Casa Sollievo della sofferenza

Manfredonia, Puglia/Foggia, 71043, Italy

NOT YET RECRUITING

Ospedale Vito Fazzi

Lecce, Puglia/Lecce, 73100, Italy

NOT YET RECRUITING

Ospedale SS.ma Annunziata

Taranto, Puglia/Taranto, 74010, Italy

RECRUITING

Ospedale Metropolitano Riuniti "Bianchi - Melacrino - Morelli

Reggio Calabria, Reggio Calabria, Italy

NOT YET RECRUITING

Arcispedale S.Maria Nuova

Reggio Emilia, Reggio Emilia, 42123, Italy

RECRUITING

Ospedale degli Infermi di Rimini, AUSL Romagna

Rimini, Rimini, 47923, Italy

NOT YET RECRUITING

Policlinico "Tor Vergata"

Roma, Roma, 00133, Italy

NOT YET RECRUITING

Policlinico Gemelli

Roma, Roma, 00136, Italy

RECRUITING

Policlinico Umberto I - Università Sapienza

Roma, Roma, 00161, Italy

NOT YET RECRUITING

Policlinico Casilino

Roma, Roma, 00169, Italy

NOT YET RECRUITING

Ospedale Sant'Andrea

Roma, Roma, 00189, Italy

NOT YET RECRUITING

San Camillo Forlanini

Roma, Roma, Italy

NOT YET RECRUITING

Ospedale S.Giovanni di Dio e Ruggì d'Aragona

Salerno, Salerno, 84131, Italy

NOT YET RECRUITING

Azienda Ospedaliera G. Brotzu

Cagliari, Sardegna/Cagliari, 09121, Italy

NOT YET RECRUITING

Azienda Ospedaliera Universitaria

Cagliari, Sardegna/Cagliari, 09124, Italy

NOT YET RECRUITING

Policlinico Rodolico

Catania, Sicilia/Catania, 95123, Italy

RECRUITING

Policlinico G. Martino

Messina, Sicilia/Messina, 98125, Italy

NOT YET RECRUITING

Policlinico P. Giaccone

Palermo, Sicilia/Palermo, 90127, Italy

NOT YET RECRUITING

Ospedale San Donato

Arezzo, Toscana/Arezzo, 52100, Italy

NOT YET RECRUITING

Azienda Ospedaliero Universitaria Careggi e Meyer

Florence, Toscana/Firenze, 50139, Italy

RECRUITING

Fondazione Toscana Gabriele Monasterio

Pisa, Toscana/Pisa, 56126, Italy

RECRUITING

Azienda Ospedaliera Universitaria Siena

Siena, Toscana/Siena, 53100, Italy

NOT YET RECRUITING

Ospedale S.Chiara

Trento, Trentino Alto Adige/Trento, 38123, Italy

NOT YET RECRUITING

Azienda sanitaria universitaria Giuliano Isontina

Trieste, Triesta, 34170, Italy

NOT YET RECRUITING

Azienda sanitaria universitaria Friuli Centrale

Udine, Udine, 33100, Italy

NOT YET RECRUITING

Ospedale di Perugia

Perugia, Umbria/Perugia, 06129, Italy

RECRUITING

Ospedale Padova

Padua, Veneto/Padova, 35128, Italy

RECRUITING

Ospedale Policlinico Sede di Borgo Roma

Verona, Veneto/Verona, 37126, Italy

NOT YET RECRUITING

Related Publications (7)

  • Nordin S, Kozor R, Medina-Menacho K, Abdel-Gadir A, Baig S, Sado DM, Lobascio I, Murphy E, Lachmann RH, Mehta A, Edwards NC, Ramaswami U, Steeds RP, Hughes D, Moon JC. Proposed Stages of Myocardial Phenotype Development in Fabry Disease. JACC Cardiovasc Imaging. 2019 Aug;12(8 Pt 2):1673-1683. doi: 10.1016/j.jcmg.2018.03.020. Epub 2018 May 16.

    PMID: 29778854BACKGROUND
  • Pieroni M, Moon JC, Arbustini E, Barriales-Villa R, Camporeale A, Vujkovac AC, Elliott PM, Hagege A, Kuusisto J, Linhart A, Nordbeck P, Olivotto I, Pietila-Effati P, Namdar M. Cardiac Involvement in Fabry Disease: JACC Review Topic of the Week. J Am Coll Cardiol. 2021 Feb 23;77(7):922-936. doi: 10.1016/j.jacc.2020.12.024.

    PMID: 33602475BACKGROUND
  • Linhart A, Germain DP, Olivotto I, Akhtar MM, Anastasakis A, Hughes D, Namdar M, Pieroni M, Hagege A, Cecchi F, Gimeno JR, Limongelli G, Elliott P. An expert consensus document on the management of cardiovascular manifestations of Fabry disease. Eur J Heart Fail. 2020 Jul;22(7):1076-1096. doi: 10.1002/ejhf.1960. Epub 2020 Aug 14.

    PMID: 32640076BACKGROUND
  • Germain DP, Hughes DA, Nicholls K, Bichet DG, Giugliani R, Wilcox WR, Feliciani C, Shankar SP, Ezgu F, Amartino H, Bratkovic D, Feldt-Rasmussen U, Nedd K, Sharaf El Din U, Lourenco CM, Banikazemi M, Charrow J, Dasouki M, Finegold D, Giraldo P, Goker-Alpan O, Longo N, Scott CR, Torra R, Tuffaha A, Jovanovic A, Waldek S, Packman S, Ludington E, Viereck C, Kirk J, Yu J, Benjamin ER, Johnson F, Lockhart DJ, Skuban N, Castelli J, Barth J, Barlow C, Schiffmann R. Treatment of Fabry's Disease with the Pharmacologic Chaperone Migalastat. N Engl J Med. 2016 Aug 11;375(6):545-55. doi: 10.1056/NEJMoa1510198.

    PMID: 27509102BACKGROUND
  • Biegstraaten M, Arngrimsson R, Barbey F, Boks L, Cecchi F, Deegan PB, Feldt-Rasmussen U, Geberhiwot T, Germain DP, Hendriksz C, Hughes DA, Kantola I, Karabul N, Lavery C, Linthorst GE, Mehta A, van de Mheen E, Oliveira JP, Parini R, Ramaswami U, Rudnicki M, Serra A, Sommer C, Sunder-Plassmann G, Svarstad E, Sweeb A, Terryn W, Tylki-Szymanska A, Tondel C, Vujkovac B, Weidemann F, Wijburg FA, Woolfson P, Hollak CE. Recommendations for initiation and cessation of enzyme replacement therapy in patients with Fabry disease: the European Fabry Working Group consensus document. Orphanet J Rare Dis. 2015 Mar 27;10:36. doi: 10.1186/s13023-015-0253-6.

    PMID: 25885911BACKGROUND
  • Ortiz A, Germain DP, Desnick RJ, Politei J, Mauer M, Burlina A, Eng C, Hopkin RJ, Laney D, Linhart A, Waldek S, Wallace E, Weidemann F, Wilcox WR. Fabry disease revisited: Management and treatment recommendations for adult patients. Mol Genet Metab. 2018 Apr;123(4):416-427. doi: 10.1016/j.ymgme.2018.02.014. Epub 2018 Feb 28.

    PMID: 29530533BACKGROUND
  • Zarate YA, Hopkin RJ. Fabry's disease. Lancet. 2008 Oct 18;372(9647):1427-35. doi: 10.1016/S0140-6736(08)61589-5.

    PMID: 18940466BACKGROUND

MeSH Terms

Conditions

Fabry Disease

Condition Hierarchy (Ancestors)

SphingolipidosesLysosomal Storage Diseases, Nervous SystemBrain Diseases, Metabolic, InbornBrain Diseases, MetabolicBrain DiseasesCentral Nervous System DiseasesNervous System DiseasesCerebral Small Vessel DiseasesCerebrovascular DisordersVascular DiseasesCardiovascular DiseasesGenetic Diseases, X-LinkedGenetic Diseases, InbornCongenital, Hereditary, and Neonatal Diseases and AbnormalitiesMetabolism, Inborn ErrorsLipidosesLipid Metabolism, Inborn ErrorsLysosomal Storage DiseasesMetabolic DiseasesNutritional and Metabolic DiseasesLipid Metabolism Disorders

Study Officials

  • Elena Biagini, MD, PhD

    IRCCS Azienda Ospedaliero-Universitaria di Bologna

    PRINCIPAL INVESTIGATOR

Central Study Contacts

Elena Biagini, MD, PhD

CONTACT

Silvia Palmieri, M. Sc.

CONTACT

Study Design

Study Type
observational
Observational Model
OTHER
Time Perspective
OTHER
Target Duration
10 Years
Sponsor Type
OTHER
Responsible Party
SPONSOR

Study Record Dates

First Submitted

January 9, 2025

First Posted

February 4, 2025

Study Start

January 26, 2022

Primary Completion (Estimated)

January 31, 2031

Study Completion (Estimated)

December 31, 2031

Last Updated

February 4, 2025

Record last verified: 2024-11

Locations