NCT06193928

Brief Summary

The objective of this 5-year, prospective, observational cohort study is to evaluate the long-term safety and clinical outcomes of patients with Alagille syndrome (ALGS) or Progressive familial intrahepatic cholestasis (PFIC) treated with Livmarli.

Trial Health

77
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
70

participants targeted

Target at P25-P50 for all trials

Timeline
53mo left

Started Sep 2023

Longer than P75 for all trials

Geographic Reach
1 country

8 active sites

Status
recruiting

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Progress38%
Sep 2023Sep 2030

Study Start

First participant enrolled

September 21, 2023

Completed
3 months until next milestone

First Submitted

Initial submission to the registry

December 11, 2023

Completed
25 days until next milestone

First Posted

Study publicly available on registry

January 5, 2024

Completed
4.7 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

September 20, 2028

Expected
2 years until next milestone

Study Completion

Last participant's last visit for all outcomes

September 20, 2030

Last Updated

May 25, 2025

Status Verified

May 1, 2025

Enrollment Period

5 years

First QC Date

December 11, 2023

Last Update Submit

May 21, 2025

Conditions

Keywords

ALGSLiver DiseasesPFICLivmarliAlagille SyndromeProgressive Familial Intrahepatic Cholestasis

Outcome Measures

Primary Outcomes (4)

  • Incidence of Long-Term Clinical Outcomes

    The dates, and reasons for the following first events (of this first endpoint) will be collected: Surgical Biliary Diversion (SBD), Liver Transplant (LT), and all-cause mortality. In addition, manifestations of clinically evident portal hypertension (CEPH) will be captured during each interval event assessments.

    Long-term clinical outcomes (SBD, LT, portal hypertension, all-cause mortality) up to 180 days after discontinuation of Livmarli will be recorded.

  • Liver Transplant Indication and Waitlist Status

    LT waitlist status will be collected, including when placed on or removed from LT waitlist.

    LT waitlist status will be collected at enrollment and every 6 months for 5 years.

  • Assessment of Growth and Development

    Height and weight will be collected both at the time the participant started Livmarli and at the time of enrollment in the study. Subsequent weight will be collected for up to 5 years. Weight z-score (kilograms) and height z-score (centimeters) will be assessed and reported every year for 5 years.

    Weight (kilograms) and height (centimeters) z-scores will be collected every year for 5 years.

  • Incidence of Clinical Events Potentially Related to Fat-Soluble Vitamin Deficiencies and Their Long-Term Sequelae

    Bleeding events (including all gastrointestinal \[GI\] or non-GI bleeding requiring hospitalization, emergency department care, or transfusion) and fracture events will be reported.

    The incidence of events will be assessed and reported every year for 5 years.

Study Arms (2)

Alagille syndrome (ALGS)

* A clinically and/or genetically confirmed ALGS diagnosis * Participant prescribed Livmarli

Drug: Livmarli

Progressive familial intrahepatic cholestasis (PFIC)

* A clinically and/or genetically confirmed PFIC diagnosis * Prescribed Livmarli

Drug: Livmarli

Interventions

The recommended dosage is 380 mcg/kg once daily.

Also known as: Maralixibat
Alagille syndrome (ALGS)

Eligibility Criteria

Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)
Sampling MethodNon-Probability Sample
Study Population

All patients with ALGS and PFIC prescribed Livmarli at a participating study center and who consent/assent to participation (if required by the local IRB/IEC) will be included in the study at the discretion of the center investigator.

You may qualify if:

  • A clinically and/or genetically confirmed ALGS diagnosis or PFIC diagnosis
  • Participant prescribed Livmarli

You may not qualify if:

  • Refusal to provide informed consent/assent (if required by the local IRB)
  • Previously or currently on Livmarli through participation in a clinical study or expanded access program
  • Participants who have previously received an SBD or LT
  • Any condition or abnormalities that, in the opinion of the investigator, may interfere with the participant participating in or completing the study
  • Participants who have received an investigational drug within 30 days of the first dose of Livmarli

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (8)

Children's Hospital Los Angeles CHLA

Los Angeles, California, 90027, United States

RECRUITING

Section of Gastroenterology, Hepatology and Nutrition, Department of Pediatrics and the Digestive Health Institute, Children's Hospital of Colorado and University of Colorado

Aurora, Colorado, 80045, United States

RECRUITING

Children's Healthcare of Atlanta - Emory University School of Medicine

Atlanta, Georgia, 30322, United States

RECRUITING

Children's Mercy Kansas City, Department of Gastroenterology, Section of Hepatology

Kansas City, Missouri, 64108, United States

RECRUITING

Oregon Health and Science University, Division of Pediatric Gastroenterology, Department of Pediatrics

Portland, Oregon, 97239, United States

RECRUITING

Children's Hospital of Philadelphia

Philadelphia, Pennsylvania, 19104, United States

RECRUITING

Children Hospital of Pittsburgh

Pittsburgh, Pennsylvania, 15260, United States

RECRUITING

University of Utah, Division of Pediatric Gastroenterology, Hepatology and Nutrition

Salt Lake City, Utah, 84112, United States

RECRUITING

Related Links

MeSH Terms

Conditions

Alagille SyndromeCholestasis, progressive familial intrahepatic 1Liver Diseases

Interventions

maralixibat

Condition Hierarchy (Ancestors)

Cholestasis, IntrahepaticCholestasisBile Duct DiseasesBiliary Tract DiseasesDigestive System DiseasesHeart Defects, CongenitalCardiovascular AbnormalitiesCardiovascular DiseasesAbnormalities, MultipleCongenital AbnormalitiesCongenital, Hereditary, and Neonatal Diseases and AbnormalitiesGenetic Diseases, Inborn

Central Study Contacts

Study Design

Study Type
observational
Observational Model
COHORT
Time Perspective
PROSPECTIVE
Target Duration
5 Years
Sponsor Type
INDUSTRY
Responsible Party
SPONSOR

Study Record Dates

First Submitted

December 11, 2023

First Posted

January 5, 2024

Study Start

September 21, 2023

Primary Completion (Estimated)

September 20, 2028

Study Completion (Estimated)

September 20, 2030

Last Updated

May 25, 2025

Record last verified: 2025-05

Locations