NCT05017155

Brief Summary

This is a clinical trial to determine if Lamotrigine is non-inferior to Mexiletine for the treatment of myotonia in patients with Non-Dystrophic Myotonia. Non-dystrophic Myotonia is a genetic condition for which there is no cure. It affects patients for the duration of their life and impacts work, leisure and can lead to significant morbidity. The study is a cross-over design - participants will be randomized to either lamotrigine or mexiletine first for 8 weeks and then swap over after a week wash-out to the other medication for a further 8 weeks. Participants and investigators will be blinded to the treatment schedule. 60 participants will recruited through the clinical service, national registry and national liaison.

Trial Health

43
At Risk

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Trial has exceeded expected completion date
Enrollment
60

participants targeted

Target at below P25 for phase_3

Timeline
Completed

Started Aug 2021

Typical duration for phase_3

Geographic Reach
1 country

1 active site

Status
unknown

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

First Submitted

Initial submission to the registry

August 11, 2021

Completed
1 day until next milestone

Study Start

First participant enrolled

August 12, 2021

Completed
11 days until next milestone

First Posted

Study publicly available on registry

August 23, 2021

Completed
1.9 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

August 1, 2023

Completed
8 months until next milestone

Study Completion

Last participant's last visit for all outcomes

April 2, 2024

Completed
Last Updated

November 2, 2022

Status Verified

November 1, 2022

Enrollment Period

2 years

First QC Date

August 11, 2021

Last Update Submit

November 1, 2022

Conditions

Outcome Measures

Primary Outcomes (1)

  • Interactive Voice Response (IVR) -diary score

    Improvement seen on the 9 point Interactive Voice Response (IVR) -diary score

    Time Frame: last two weeks of each treatment period - [Minimum value 0- no myotonia. Maximum value 9 - severe myotonia].

Secondary Outcomes (6)

  • Secondary Outcome - Timed up and go

    end of each treatment period (two months)

  • Secondary Outcome - Timed sit to stand

    end of each treatment period (two months)

  • Fatigue Scale

    end of each treatment period (two months)

  • Secondary Outcome

    end of each treatment period (two months)

  • Short-Form Health Survey (SF-36)

    end of each treatment period (two months)

  • +1 more secondary outcomes

Study Arms (2)

Lamotrigine

ACTIVE COMPARATOR

When on the lamotrigine treatment arm, the participant will commence at lamotrigine 25mg (milligram) daily for two weeks; then increase to 25mg twice daily for two weeks; then increase to 50mg daily for one week; then increase to 100mg in the morning, 50mg at midday and 50mg at night for one week; then increase to 100mg in the morning, 50mg at midday and 100mg at night for two weeks.

Drug: MexiletineDrug: Lamotrigine 25Mg Oral Tablet, Extended Release

Mexiletine

ACTIVE COMPARATOR

When on the mexiletine treatment arm, the participant will commence at mexiletine 100mg daily for two weeks; then increase to 200mg daily for two weeks; then increase to 200mg twice daily for one week; then increase to 200mg three times a day for one week; then remain on 200mg three times a day for two weeks.

Drug: MexiletineDrug: Lamotrigine 25Mg Oral Tablet, Extended Release

Interventions

Mexiletine is a sodium channel blocker shown to be effective in reducing myotonia in a multi-centre randomised trial.

LamotrigineMexiletine

Lamotrigine is an alternative sodium channel blocker that has been shown to be effective in one randomised controlled trial. It is currently used as a licensed medication for other neurological conditions.

LamotrigineMexiletine

Eligibility Criteria

Age18 Years - 90 Years
Sexall
Healthy VolunteersNo
Age GroupsAdult (18-64), Older Adult (65+)

You may qualify if:

  • adults (≥ 18years),
  • genetically confirmed non-dystrophic myotonia (NDM),
  • presence of symptomatic myotonia as reported by the participant.

You may not qualify if:

  • concomitant medical conditions that would preclude the use of mexiletine or lamotrigine,
  • evidence of severe kidney disease or severe liver impairment \[estimated glomerular filtration rate (eGFR) as calculated by the Chronic Kidney Disease Epidemiology Collaboration (CKD-EPI) Creatinine Equation \<60ml/min/1.73m2\],
  • pregnant or breastfeeding women,
  • participation in other treatment studies \<30days before enrolment.

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (1)

University College London Hospital

London, WC1N 3BG, United Kingdom

RECRUITING

Related Publications (1)

  • Vivekanandam V, Skorupinska I, Jayaseelan DL, Matthews E, Barohn RJ, McDermott MP, Hanna MG. Mexiletine versus lamotrigine in non-dystrophic myotonias: a randomised, double-blind, head-to-head, crossover, non-inferiority, phase 3 trial. Lancet Neurol. 2024 Oct;23(10):1004-1012. doi: 10.1016/S1474-4422(24)00320-X.

MeSH Terms

Interventions

MexiletineLamotrigineTablets

Intervention Hierarchy (Ancestors)

PropylaminesAminesOrganic ChemicalsPhenyl EthersPhenolsBenzene DerivativesHydrocarbons, AromaticHydrocarbons, CyclicHydrocarbonsTriazinesHeterocyclic Compounds, 1-RingHeterocyclic CompoundsDosage FormsPharmaceutical Preparations

Central Study Contacts

Vinojini Vivekanandam, Dr

CONTACT

Iwona Skorupinska, Nurse

CONTACT

Study Design

Study Type
interventional
Phase
phase 3
Allocation
RANDOMIZED
Masking
QUADRUPLE
Who Masked
PARTICIPANT, CARE PROVIDER, INVESTIGATOR, OUTCOMES ASSESSOR
Purpose
TREATMENT
Intervention Model
CROSSOVER
Model Details: Participants will be recruited from University College London Hospital (UCLH). After screening and consent, randomisation will occur to one of two arms. The participant will participate in two consecutive time periods. A time period will consist of 8 weeks of Mexiletine or Lamotrigine. The second time period will then occur after 7 days of washout. The patient will then take the alternative drug. Visits will occur at the end of each period and can be undertaken remotely as required. At each visit, the Interactive Voice Response (IVR)-Diary score will be performed and secondary measures including the Brief Pain Inventory, Modified Fatigue Severity Scale and Medical Outcomes Study Questionnaire (SF-36). Objective recordings including Timed up and Go (TUG), Timed Sit to Stand (TST). Safety data will be recorded simultaneously. A participant diary will be utilised to record daily IVR-Diary scores, medication compliance and activity measures.
Sponsor Type
OTHER
Responsible Party
SPONSOR

Study Record Dates

First Submitted

August 11, 2021

First Posted

August 23, 2021

Study Start

August 12, 2021

Primary Completion

August 1, 2023

Study Completion

April 2, 2024

Last Updated

November 2, 2022

Record last verified: 2022-11

Data Sharing

IPD Sharing
Will not share

Request for sharing anonymised data can be made to the Chief Investigator (CI) for discussion/consideration.

Locations