NCT04248465

Brief Summary

The purpose of the study is to assess the efficacy and safety of ravulizumab for the treatment of adult participants with ALS.

Trial Health

68
Monitor

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
382

participants targeted

Target at P50-P75 for phase_3

Timeline
Completed

Started Mar 2020

Geographic Reach
17 countries

95 active sites

Status
terminated

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

First Submitted

Initial submission to the registry

January 27, 2020

Completed
3 days until next milestone

First Posted

Study publicly available on registry

January 30, 2020

Completed
2 months until next milestone

Study Start

First participant enrolled

March 30, 2020

Completed
1.6 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

October 17, 2021

Completed
Same day until next milestone

Study Completion

Last participant's last visit for all outcomes

October 17, 2021

Completed
1.2 years until next milestone

Results Posted

Study results publicly available

January 10, 2023

Completed
Last Updated

January 10, 2023

Status Verified

December 1, 2022

Enrollment Period

1.6 years

First QC Date

January 27, 2020

Results QC Date

September 22, 2022

Last Update Submit

December 15, 2022

Conditions

Keywords

RavulizumabALXN1210UltomirisMotor Neuron DiseaseAmyotrophic Lateral SclerosisALS

Outcome Measures

Primary Outcomes (1)

  • Change From Baseline In Amyotrophic Lateral Sclerosis Functional Rating Scale-Revised (ALSFRS-R) Total Score

    The ALSFRS-Revised is a validated instrument for evaluating the levels of the functional status of participants with amyotrophic lateral sclerosis (ALS) in 4 areas, including bulbar, gross motor activity, fine motor activity, and respiratory functions. The scale included 12 functional items and each item is rated on a 0 to 4 scale, with a maximum total score of 48. A higher score indicated greater retention of function. Baseline was defined as last non-missing value on or before first study drug administration.

    Baseline, Week 50

Secondary Outcomes (8)

  • Time To Ventilator Assistance-free Survival

    Up to Week 50

  • Change From Baseline In Percent Predicted Slow Vital Capacity

    Baseline, Week 50

  • Number of Participants With Treatment-emergent Adverse Events (TEAEs), Treatment-emergent Serious Adverse Events, and TEAEs Leading To Study Drug Discontinuation

    Baseline up to Week 156

  • Change From Baseline In Muscle Strength As Assessed By Handheld Dynamometry

    Baseline, Week 50

  • Change From Baseline In Serum Neurofilament Light Chain

    Baseline, Week 50

  • +3 more secondary outcomes

Study Arms (2)

Ravulizumab

EXPERIMENTAL

Participants will receive ravulizumab for the duration of the study.

Biological: Ravulizumab

Placebo

PLACEBO COMPARATOR

Participants will receive placebo during the 50-week Randomized Controlled Period of the study, after which they will enter the Open-label Extension Period of the study and switch to receive ravulizumab.

Drug: PlaceboBiological: Ravulizumab

Interventions

Single loading dose via intravenous infusion, followed by regular maintenance dosing, based on weight.

Placebo
RavulizumabBIOLOGICAL

Single loading dose via intravenous infusion, followed by regular maintenance dosing, based on weight.

Also known as: ALXN1210, Ultomiris
PlaceboRavulizumab

Eligibility Criteria

Age18 Years+
Sexall
Healthy VolunteersNo
Age GroupsAdult (18-64), Older Adult (65+)

You may qualify if:

  • A diagnosis of sporadic or familial ALS, defined by the El Escorial criteria (possible, laboratory-supported probable, probable, or definite ALS).
  • ALS onset ≤ 36 months from Screening.
  • Documented meningococcal vaccination not more than 3 years prior to, or at the time of, initiating study treatment.
  • Upright slow vital capacity ≥ 65% predicted at Screening.
  • If on riluzole, participant must be on a stable dose for 30 days; if on edaravone, participant must be on a stable dose for 60 days (2 cycles).
  • Body weight ≥ 40 kilograms at Screening.
  • Contraceptive use by men or women should be consistent with local regulations regarding the methods of contraception for those participating in clinical studies.

You may not qualify if:

  • History of Neisseria meningitidis infection.
  • Human immunodeficiency virus (HIV) infection (evidenced by HIV 1 or HIV 2 antibody titer).
  • Dependence on invasive or non-invasive mechanical ventilation.
  • Previously or currently treated with a complement inhibitor.
  • Exposure to an investigational drug or device within 30 days of Screening or 5 half lives of the study drug, whichever is greater.

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (95)

Barrow Neurological Institute

Phoenix, Arizona, 85013, United States

Location

Neuromuscular Research Center and Clinic

Phoenix, Arizona, 85028, United States

Location

HonorHealth Research Institute

Scottsdale, Arizona, 85251, United States

Location

Loma Linda University Medical Center

Loma Linda, California, 92354, United States

Location

University of Southern California

Los Angeles, California, 90033, United States

Location

University of California-Irvine

Orange, California, 92868, United States

Location

Stanford University Medical Center

Palo Alto, California, 94304, United States

Location

University of California San Diego Medical Center

San Diego, California, 92093-0949, United States

Location

Norris MDA/ALS Center

San Francisco, California, 94115, United States

Location

University of California San Francisco Medical Center

San Francisco, California, 94143, United States

Location

University of Colorado Anschutz Medical Campus School of Medicine

Aurora, Colorado, 80045, United States

Location

University of Florida at Shands Jacksonville

Jacksonville, Florida, 32209, United States

Location

University of South Florida

Tampa, Florida, 33612, United States

Location

University of Chicago Medical Center

Chicago, Illinois, 60637, United States

Location

Indiana University Medical Center

Indianapolis, Indiana, 46202, United States

Location

University of Kansas Medical Center Research Institute, Inc.

Kansas City, Kansas, 66160, United States

Location

University of Kentucky

Lexington, Kentucky, 40536, United States

Location

Johns Hopkins University School Of Medicine

Baltimore, Maryland, 21205, United States

Location

Massachusetts General Hospital

Boston, Massachusetts, 02114, United States

Location

Las Vegas Clinic

Las Vegas, Nevada, 89145, United States

Location

Beth Israel Medical Center - PRIME

New York, New York, 10003, United States

Location

Hospital for Special Surgery

New York, New York, 10021, United States

Location

Atrium Health Neuroscience Institute

Charlotte, North Carolina, 28207, United States

Location

The Cleveland Clinic Foundation

Cleveland, Ohio, 44195, United States

Location

The Ohio State University

Columbus, Ohio, 43221, United States

Location

Allegheny Neurological Associates

Pittsburgh, Pennsylvania, 15212, United States

Location

Vanderbilt University Medical Center

Nashville, Tennessee, 37232, United States

Location

Austin Neuromuscular Center

Austin, Texas, 78756, United States

Location

Houston Methodist Neurological Institute-Movement Disorders Clinic

Houston, Texas, 77030, United States

Location

Nerve & Muscle Center of Texas

Houston, Texas, 77030, United States

Location

University of Vermont Medical Center

Burlington, Vermont, 05401, United States

Location

Virginia Commonwealth University, Neurology Clinical and Translational Research Office

Richmond, Virginia, 23298, United States

Location

Sentara Neurology Specialists

Virginia Beach, Virginia, 23456, United States

Location

Swedish Neuroscience Institute

Seattle, Washington, 98122-4470, United States

Location

Brain and Mind Centre

Camperdown, New South Wales, 2050, Australia

Location

Westmead Hospital

Westmead, New South Wales, 2145, Australia

Location

Royal Brisbane and Women's Hospital

Herston, Queensland, 4029, Australia

Location

Perron Institute for Neurological and Translational Science

Nedlands, Western Australia, 6009, Australia

Location

UZ Leuven

Leuven, 3000, Belgium

Location

Heritage Medical Research Centre (HMRC)

Edmonton, Alberta, T6G2S2, Canada

Location

Stan Cassidy Center for Rehabilitation

Fredericton, New Brunswick, E3B 0C7, Canada

Location

LHSC - University Hospital

London, Ontario, N6A 5A5, Canada

Location

Toronto Sunnybrook Hospital

Toronto, Ontario, M4N 3M5, Canada

Location

Montreal Neurological Institute and Hospital

Montreal, Quebec, H3A 2B4, Canada

Location

University Hospital of Quebec-Universite Laval

Québec, Quebec, G1J 1Z4, Canada

Location

Royal University Hospital

Saskatoon, Saskatchewan, S7K 0M7, Canada

Location

Ålborg Universitets Hospital

Aalborg, 9100, Denmark

Location

Aarhus University Hospital Department of Neurology

Aarhus, 8200, Denmark

Location

Bispebjerg Hospital

Copenhagen, 2400, Denmark

Location

CHU de Nice Hôpital Pasteur 2

Nice, Alpes Maritimes, 06001, France

Location

CHU de Limoges - Hôpital Dupuytren

Limoges, Haute Vienne, 87042, France

Location

Hopital Gui de Chauliac

Montpellier, Herault, 34295, France

Location

CHU Tours - Hôpital Bretonneau

Tours, Indre Et Loire, 37044, France

Location

Hopital Neurologique Pierre Wertheimer

Bron, Rhone, 69677, France

Location

Hopital Roger Salengro - CHU Lille

Lille, 59037, France

Location

Hôpital de la Timone

Marseille, 13385, France

Location

Groupe Hospitalier Pitie-Salpetriere

Paris, 75651, France

Location

Universitaetsklinikum Ulm

Ulm, Baden-Wurttemberg, 89081, Germany

Location

Klinikum rechts der Isar der TU Muenchen

Munich, Bavaria, 81675, Germany

Location

Universitaetsmedizin Goettingen

Goettigen, Lower Saxony, 37099, Germany

Location

Medizinische Hochschule Hannover

Hanover, Lower Saxony, 30625, Germany

Location

Universitaetsklinikum Jena

Jena, Thuringia, 07749, Germany

Location

Beaumont Hospital

Dublin, DUBLIN 9, Ireland

Location

Rambam Health Care Center

Haifa, 91096, Israel

Location

Hadassah University Hospital - Ein Kerem

Jerusalem, 91120, Israel

Location

Tel Aviv Sourasky Medical Center

Tel Aviv, 6423906, Israel

Location

Ospedale San Raffaele

Milan, 20132, Italy

Location

ICS Maugeri IRCCS

Milan, 20138, Italy

Location

Istituto Auxologico Italiano

Milan, 20149, Italy

Location

Azienda Ospedaliero-Universitaria di Modena - Ospedale Civile di Baggiovara

Modena, 1355 - 41126, Italy

Location

Azienda Ospedaliero Universitaria Policlinico Paolo Giaccone

Palermo, 90127, Italy

Location

Azienda Ospedaliero Universitaria Pisana

Pisa, 56126, Italy

Location

University of Turin

Torino, 10126, Italy

Location

Nagoya University Hospital

Nagoya, Aichi-ken, 466-8560, Japan

Location

Chiba University Hospital

Chiba, Chiba, 260-8677, Japan

Location

Yoshino Neurology Clinic

Ichikawa-shi, Chiba, 272-0827, Japan

Location

Tohoku University Hospital

Sendai, Miyagi, 980-8574, Japan

Location

Niigata University Medical & Dental Hospital

Niigata, Niigata, 951-8520, Japan

Location

Shiga University of Medical Science Hospital

Ōtsu, Shiga, 520-2192, Japan

Location

Tokushima University Hospital

Tokushima, Tokushima, 770-8503, Japan

Location

Medical Hospital, Tokyo Medical and Dental University

Bunkyō City, Tokyo-To, 113-8519, Japan

Location

Toho University Omori Medical Center

Ōta-ku, Tokyo-To, 143-8541, Japan

Location

Keio University Hospital

Shinjuku-Ku, Tokyo-To, 160-8582, Japan

Location

University Medical Centre Utrecht

Utrecht, 3508 GA, Netherlands

Location

CityClinic

Warsaw, 02-473, Poland

Location

Hospital Universitari de Bellvitge

L'Hospitalet de Llobregat, Barcelona, 08907, Spain

Location

Hospital de la Santa Creu i Sant Pau

Barcelona, 08025, Spain

Location

Hospital Universitari Vall d'Hebron

Barcelona, 08035, Spain

Location

Hospital San Rafael

Madrid, 28016, Spain

Location

Hospital Universitari i Politecnic La Fe

Valencia, 46026, Spain

Location

Karolinska Trial Alliance (KTA)

Huddinge, 141 86, Sweden

Location

Norrlands universitetssjukhus

Umeå, 90185, Sweden

Location

Kantonsspital St. Gallen

Sankt Gallen, 9007, Switzerland

Location

The National Hospital for Neurology & Neurosurgery

London, Greater London, WC1N 3BG, United Kingdom

Location

Royal Hallamshire Hospital

Sheffield, West Midlands, S10 2JF, United Kingdom

Location

Related Publications (1)

  • Genge A, van den Berg LH, Frick G, Han S, Abikoff C, Simmons A, Lin Q, Patra K, Kupperman E, Berry JD. Efficacy and Safety of Ravulizumab, a Complement C5 Inhibitor, in Adults With Amyotrophic Lateral Sclerosis: A Randomized Clinical Trial. JAMA Neurol. 2023 Oct 1;80(10):1089-1097. doi: 10.1001/jamaneurol.2023.2851.

MeSH Terms

Conditions

Amyotrophic Lateral SclerosisMotor Neuron Disease

Interventions

ravulizumab

Condition Hierarchy (Ancestors)

Spinal Cord DiseasesCentral Nervous System DiseasesNervous System DiseasesNeurodegenerative DiseasesTDP-43 ProteinopathiesNeuromuscular DiseasesProteostasis DeficienciesMetabolic DiseasesNutritional and Metabolic Diseases

Limitations and Caveats

The IDMC recommended the study be discontinued due to lack of efficacy with ravulizumab.

Results Point of Contact

Title
Alexion Pharmaceuticals Inc.
Organization
Alexion Pharmaceuticals Inc.

Publication Agreements

PI is Sponsor Employee
No
Restrictive Agreement
Yes

Study Design

Study Type
interventional
Phase
phase 3
Allocation
RANDOMIZED
Masking
QUADRUPLE
Who Masked
PARTICIPANT, CARE PROVIDER, INVESTIGATOR, OUTCOMES ASSESSOR
Purpose
TREATMENT
Intervention Model
PARALLEL
Sponsor Type
INDUSTRY
Responsible Party
SPONSOR

Study Record Dates

First Submitted

January 27, 2020

First Posted

January 30, 2020

Study Start

March 30, 2020

Primary Completion

October 17, 2021

Study Completion

October 17, 2021

Last Updated

January 10, 2023

Results First Posted

January 10, 2023

Record last verified: 2022-12

Locations