NCT03424772

Brief Summary

To assess the indications and diagnostic efficiency of whole genome sequencing (WGS) in pediatric patients with unexplained intellectual disability/developmental delay, multiple congenital abnormalities and other rare and undiagnosed diseases

Trial Health

43
At Risk

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Trial has exceeded expected completion date
Enrollment
100

participants targeted

Target at P50-P75 for all trials

Timeline
Completed

Started Jan 2018

Geographic Reach
1 country

14 active sites

Status
unknown

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Start

First participant enrolled

January 18, 2018

Completed
12 days until next milestone

First Submitted

Initial submission to the registry

January 30, 2018

Completed
8 days until next milestone

First Posted

Study publicly available on registry

February 7, 2018

Completed
10 months until next milestone

Primary Completion

Last participant's last visit for primary outcome

December 1, 2018

Completed
3 months until next milestone

Study Completion

Last participant's last visit for all outcomes

March 1, 2019

Completed
Last Updated

February 8, 2018

Status Verified

February 1, 2018

Enrollment Period

11 months

First QC Date

January 30, 2018

Last Update Submit

February 6, 2018

Conditions

Outcome Measures

Primary Outcomes (1)

  • Number of diagnosed families

    Families with rare and undiagnosed pediatric genetic disease will be benefitted by WGS.

    1 year

Secondary Outcomes (1)

  • Numbers of pathogenic variants in different variation types

    1 year

Study Arms (1)

Patients with unexplained DD/ID

Whole genome sequencing will be performed on pediatric patients with unexplained developmental delay(DD)/intellectual disability(ID), multiple congenital abnormalities and other rare and undiagnosed diseases.

Diagnostic Test: Whole genome sequencing

Interventions

WGS will be performed for the trio

Patients with unexplained DD/ID

Eligibility Criteria

AgeUp to 18 Years
Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64)
Sampling MethodNon-Probability Sample
Study Population

Undiagnosed Children with intellectual disability/developmental delay and/or multiple congenital abnormalites in China

You may qualify if:

  • Intelligence tests results of less than 40 (patients \<3 years old using the Gesell Developmental Scale for screening; patients of 3-6 years old using Little Wechsler Intelligence Scale for screening; patients \>6 years old using Old Wechsler Intelligence Scale for screening).
  • Neurodevelopmental defects can be expressed as mental retardation, motor development retardation, language delay, epilepsy, etc. May have or not have Multiple congenital abnormalities, families with more than one affected patient will be enrolled priority
  • Families went through at least one of the high throughput technology(WES or CMA) and receive the negative result

You may not qualify if:

  • Intellectual disability caused by pregnancy, perinatal infection, ischemia, and hypoxia and other non-hereditary causes,
  • Obvious genetic metabolic diseases (such as different types of genetic metabolic diseases, bone disease, fragile X syndrome, etc.);

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (14)

Peking Union Medical College Hospital

Beijing, Beijing Municipality, 100005, China

RECRUITING

Children's Hospital, Capital Institute of Pediatrics

Beijing, Beijing Municipality, 100020, China

RECRUITING

Department of Pediatrics, Peking University First Hospital

Beijing, Beijing Municipality, 100034, China

RECRUITING

The Maternal & Child Health Hospital, The Children's Hospital, The Obstetrics & Gynecology Hospital of Guangxi Zhuang Autonomous Region

Nanning, Guangxi, 530005, China

RECRUITING

The Maternal and Child Health Hospital of Hunan Province

Changsha, Hunan, 410008, China

RECRUITING

Xiangya Hospital, Central-south University / Hunan Jiahui genetics hospital

Changsha, Hunan, 410008, China

RECRUITING

Hunan Children's Hospital

Changsha, Hunan, 410011, China

RECRUITING

Nanjing maternal and children hospital

Nanjing, Jiangsu, 210004, China

RECRUITING

Ruijin Hospital affiliated to Shanghai Jiaotong University

Shanghai, Shanghai Municipality, 200025, China

RECRUITING

Children's Hospital of Shanghai

Shanghai, Shanghai Municipality, 200041, China

RECRUITING

Shanghai Institute for Pediatric Research

Shanghai, Shanghai Municipality, 200092, China

RECRUITING

Xin Hua Hospital, Shanghai Jiaotong University School of Medicine

Shanghai, Shanghai Municipality, 200092, China

RECRUITING

Shanghai Children's Medical Center

Shanghai, Shanghai Municipality, 201712, China

RECRUITING

Wenzhou Central Hospital

Wenzhou, Zhejiang, 325099, China

RECRUITING

Related Publications (1)

  • Park ST, Kim J. Trends in Next-Generation Sequencing and a New Era for Whole Genome Sequencing. Int Neurourol J. 2016 Nov;20(Suppl 2):S76-83. doi: 10.5213/inj.1632742.371. Epub 2016 Nov 22.

    PMID: 27915479BACKGROUND

Related Links

Biospecimen

Retention: SAMPLES WITH DNA

Genomic DNA will be extracted from whole blood

MeSH Terms

Conditions

Intellectual DisabilityAbnormalities, MultipleRare Diseases

Condition Hierarchy (Ancestors)

Neurobehavioral ManifestationsNeurologic ManifestationsNervous System DiseasesSigns and SymptomsPathological Conditions, Signs and SymptomsNeurodevelopmental DisordersMental DisordersCongenital AbnormalitiesCongenital, Hereditary, and Neonatal Diseases and AbnormalitiesDisease AttributesPathologic Processes

Study Officials

  • Yongguo Yu, MD, PhD

    Specify Unaffiliated

    PRINCIPAL INVESTIGATOR

Central Study Contacts

Study Design

Study Type
observational
Observational Model
FAMILY BASED
Time Perspective
PROSPECTIVE
Target Duration
1 Year
Sponsor Type
OTHER
Responsible Party
PRINCIPAL INVESTIGATOR
PI Title
Associate chief physician

Study Record Dates

First Submitted

January 30, 2018

First Posted

February 7, 2018

Study Start

January 18, 2018

Primary Completion

December 1, 2018

Study Completion

March 1, 2019

Last Updated

February 8, 2018

Record last verified: 2018-02

Locations