NCT03193476

Brief Summary

This is an international, multicentre, prospective, non-interventional, observational Registry of patients with X-Linked hypophosphatemia (XLH). The main objective of this XLH Registry is to collect data to characterise the treatment, progression and long-term outcomes of XLH in both adult and paediatric settings.

Trial Health

88
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Strong global presence with extensive site network
Enrollment
1,343

participants targeted

Target at P75+ for all trials

Timeline
39mo left

Started Sep 2017

Longer than P75 for all trials

Geographic Reach
19 countries

117 active sites

Status
recruiting

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Progress73%
Sep 2017Jul 2029

First Submitted

Initial submission to the registry

June 13, 2017

Completed
7 days until next milestone

First Posted

Study publicly available on registry

June 20, 2017

Completed
3 months until next milestone

Study Start

First participant enrolled

September 12, 2017

Completed
11.4 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

February 1, 2029

Expected
5 months until next milestone

Study Completion

Last participant's last visit for all outcomes

July 1, 2029

Last Updated

September 19, 2024

Status Verified

September 1, 2024

Enrollment Period

11.4 years

First QC Date

June 13, 2017

Last Update Submit

September 4, 2024

Conditions

Keywords

CrysvitaBurosumabX-linked Hypophosphatemia (XLH)PHEX Gene MutationXLH Registry

Outcome Measures

Primary Outcomes (1)

  • Number of participants with treatment-related adverse events as assessed by CTCAE v4.0

    Number of participants with treatment-related adverse events as assessed by CTCAE v4.0

    10 years

Eligibility Criteria

Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)
Sampling MethodNon-Probability Sample
Study Population

Patients with XLH independent of treatment regimen

You may qualify if:

  • Patients aged from ≥0 years of age at baseline
  • In the opinion of the treating physician the patient has a clinical presentation, radiological, biochemical or genetic investigation results that support diagnosis of XLH
  • Patient is not currently participating in an interventional clinical trial
  • A patient who meets any of the following criteria at the enrolment visit (baseline) will be excluded from this XLH Registry

You may not qualify if:

  • Patient or their legally designated representative does not have the cognitive capacity to provide informed consent.
  • Participation in a Compassionate Use Program, Pre-commercial Program (i.e. Named Patient Sales, Nominative ATU) or Investigator Initiated Study does not preclude a patient from participation in this XLH Registry

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (118)

Hopital Universitaire des Enfants Reine Fabiola

Brussels, 1020, Belgium

RECRUITING

Universitair Ziekenhuis Brussel

Brussels, 1090, Belgium

RECRUITING

Cliniques Universitaires Saint-Luc

Brussels, 1200, Belgium

RECRUITING

UZA

Edegem, 2650, Belgium

RECRUITING

Universitair Ziekenhuis Gent

Ghent, 9000, Belgium

RECRUITING

UZ Leuven

Leuven, 3000, Belgium

RECRUITING

CHU de Liège

Liège, 4000, Belgium

RECRUITING

SHATPD "Prof Ivan Mitev" EAD

Sofia, 1606, Bulgaria

ACTIVE NOT RECRUITING

UMHAT "SofiaMed", OOD

Sofia, 1797, Bulgaria

ACTIVE NOT RECRUITING

Children Hospital

Brno, 625 00, Czechia

ACTIVE NOT RECRUITING

Fakultni nemocnice v Motole

Prague, 150 06, Czechia

ACTIVE NOT RECRUITING

Aalborg University Hospital

Aalborg, 9100, Denmark

ACTIVE NOT RECRUITING

Århus Universitetshospital - Aarhus sygehus

Aarhus, 8200, Denmark

ACTIVE NOT RECRUITING

Århus Universitetshospital

Aarhus, 8200, Denmark

ACTIVE NOT RECRUITING

Hospital South West Jutland

Esbjerg, 6700, Denmark

COMPLETED

Rigshospitalet - Paediatric

København Ø, 2100, Denmark

ACTIVE NOT RECRUITING

Rigshospitalet

København Ø, 2100, Denmark

COMPLETED

OUH

Odense, 5000, Denmark

ACTIVE NOT RECRUITING

Groupe Hospitalier Pellegrin - Hôpital des Enfants

Bordeaux, 33000, France

ACTIVE NOT RECRUITING

CHU de Lyon - Hôpital Femme Mere Enfant

Bron, 69677, France

ACTIVE NOT RECRUITING

CHRU Lille

Lille, 59037, France

ACTIVE NOT RECRUITING

Hopital Roger Salengro - CHU Lille

Lille, 59037, France

ACTIVE NOT RECRUITING

Hopital Arnaud de Villeneuve

Montpellier, 34295, France

ACTIVE NOT RECRUITING

CHU de Nantes

Nantes, 44000, France

NOT YET RECRUITING

Hôpital Cochin

Paris, 75679, France

ACTIVE NOT RECRUITING

CHU Paris Sud - Hopital Bicêtre

Paris, 94270, France

ACTIVE NOT RECRUITING

Hôpital Bicêtre

Paris, 94275, France

ACTIVE NOT RECRUITING

"Hopital Pierre-Paul Riquet Centre de Rhumatologie"

Toulouse, 31059, France

ACTIVE NOT RECRUITING

Hopital Purpan

Toulouse, 31059, France

ACTIVE NOT RECRUITING

Klinikum Ernst-von-Bergmann Potsdam und Bad Belzig

Bad Belzig, Germany

ACTIVE NOT RECRUITING

Uniklinikum Bochum

Bochum, 44791, Germany

WITHDRAWN

Uniklinikum Koeln

Cologne, 50937, Germany

WITHDRAWN

MVZ Dr. Eberhard & Partner

Dortmund, 44137, Germany

WITHDRAWN

Universitaetsklinikum Freiburg

Freiburg im Breisgau, 79106, Germany

WITHDRAWN

Medizinische Hochschule Hannover

Hanover, 30625, Germany

ACTIVE NOT RECRUITING

Universitaetsklinikum

Leipzig, 04103, Germany

ACTIVE NOT RECRUITING

Hormon and Stoffwechselzentrum

Mainz, 55122, Germany

ACTIVE NOT RECRUITING

Semmelweis Egyetem

Budapest, 1083, Hungary

ACTIVE NOT RECRUITING

Semmelweis Egyetem

Budapest, 1085, Hungary

ACTIVE NOT RECRUITING

The Children's University Hospital

Dublin, DO1 XD99, Ireland

ACTIVE NOT RECRUITING

Rambam Health Care Center

Haifa, 3109601, Israel

ACTIVE NOT RECRUITING

Schneider Medical Center

Petah Tikva, 4920235, Israel

ACTIVE NOT RECRUITING

Sheba Medical Center

Ramat Gan, 5265601, Israel

ACTIVE NOT RECRUITING

Dana-Dwek Children's Hospital

Tel Aviv, 64239, Israel

WITHDRAWN

Azienda Ospedaliero Universitaria Consorziale Policlinico di Bari

Bari, 70124, Italy

ACTIVE NOT RECRUITING

AO S. Pio G. Rumno

Benevento, 82100, Italy

ACTIVE NOT RECRUITING

Azienda Ospedaliera Universitaria Policlinico Sant'Orsola Malpighi

Bologna, 40138, Italy

ACTIVE NOT RECRUITING

Presidio Ospedaliero Di Summa Antonio Perrino

Brindisi, 72100, Italy

ACTIVE NOT RECRUITING

Azienda Ospedaliera Brotzu

Cagliari, 09121, Italy

ACTIVE NOT RECRUITING

Azienda Ospedaliera Universitaria Careggi

Florence, 50134, Italy

ACTIVE NOT RECRUITING

Istituto Giannina Gaslini-Ospedale Pediatrico IRCCS

Genova, 16147, Italy

ACTIVE NOT RECRUITING

ICOT-Istituto Chirurgico Ortopedico Traumatologico

Latina, 04100, Italy

NOT YET RECRUITING

Azienda Ospedaliera Universitaria Policlinico G. Martino

Messina, 98125, Italy

ACTIVE NOT RECRUITING

Ospedale San Raffaele - Adult

Milan, 20132, Italy

ACTIVE NOT RECRUITING

Ospedale San Raffaele

Milan, 20132, Italy

ACTIVE NOT RECRUITING

Azienda Ospedaliera di Padova

Padua, 35100, Italy

ACTIVE NOT RECRUITING

Azienda Ospedaliera di Padova

Padua, 35128, Italy

ACTIVE NOT RECRUITING

Istituto Auxologico Italiano -I.R.C.C.S.

Piancavallo, 20145, Italy

ACTIVE NOT RECRUITING

Stabilimento Ospedaliero Santa Chiara

Pisa, 56100, Italy

ACTIVE NOT RECRUITING

Ospedale Pediatrico Bambino Gesù

Roma, 00165, Italy

ACTIVE NOT RECRUITING

Azienda Ospedaliera Città della Salute e della Scienza di Torino (Presidio Sant'Anna)

Torino, 10126, Italy

NOT YET RECRUITING

Azienda Ospedaliero-Universitaria Città della Salute e della Scienza di Torino

Torino, 10126, Italy

ACTIVE NOT RECRUITING

I.R.C.C.S. Burlo Garofolo

Trieste, 34137, Italy

ACTIVE NOT RECRUITING

Children's Clinical University Hospital

Riga, LV-1002, Latvia

ACTIVE NOT RECRUITING

Universitair Medisch Centrum Groningen

Groningen, 9713 GZ, Netherlands

ACTIVE NOT RECRUITING

Oslo University Hospital

Oslo, 0424, Norway

ACTIVE NOT RECRUITING

Oslo Universitetssykehus HF, Ulleval

Oslo, 0450, Norway

ACTIVE NOT RECRUITING

St. Olav's University Hospital

Trondheim, 7030, Norway

ACTIVE NOT RECRUITING

Hospital Pediatrico de Coimbra

Coimbra, 3030, Portugal

ACTIVE NOT RECRUITING

Centro Hospitalar de Lisboa Central, E.P.E. - Hospital Dona Estefânia

Lisbon, 1169-045, Portugal

ACTIVE NOT RECRUITING

Centro Hospitalar de Lisboa Norte, E.P.E. - Hospital de Santa Maria

Lisbon, 1649-035, Portugal

ACTIVE NOT RECRUITING

Centro Hospitalar do Porto, E.P.E. - Hospital de Santo António

Porto, 4099-001, Portugal

ACTIVE NOT RECRUITING

Hospital de Sao Joao

Porto, 4200-319, Portugal

ACTIVE NOT RECRUITING

National Institute of Childrenś Health NUDCH

Bratislava, 83340, Slovakia

ACTIVE NOT RECRUITING

University Clinical Centre Ljubljana

Ljubljana, Slovenia

ACTIVE NOT RECRUITING

Hospital de Cruces

Barakaldo, 48903, Spain

ACTIVE NOT RECRUITING

Hospital Universitari Vall d'Hebron

Barcelona, 08035, Spain

ACTIVE NOT RECRUITING

Hospital Clinic de Barcelona

Barcelona, 08036, Spain

ACTIVE NOT RECRUITING

Hospital General Universitario Santa Lucía

Cartagena, 30202, Spain

ACTIVE NOT RECRUITING

Hospital Universitario Virgen de la Arrixaca

El Palmar, 30120, Spain

ACTIVE NOT RECRUITING

Hospital Sant Joan de Deu

Esplugues de Llobregat, 08950, Spain

ACTIVE NOT RECRUITING

Complejo Hospitalario Universitario Insular Materno-Infantil

Las Palmas de Gran Canaria, 35016, Spain

ACTIVE NOT RECRUITING

Hospital Infantil Universitario Niño Jesus

Madrid, 28009, Spain

ACTIVE NOT RECRUITING

Hospital Universitario Central de Asturias

Oviedo, 33006, Spain

ACTIVE NOT RECRUITING

Hospital Central de Asturias

Oviedo, 33011, Spain

ACTIVE NOT RECRUITING

Hospital Universitario Nuestra Señora de la Candelaria

Santa Cruz de Tenerife, 38010, Spain

ACTIVE NOT RECRUITING

Queen Silvia Children's Hospital

Gothenburg, 416 85, Sweden

ACTIVE NOT RECRUITING

Lund University

Lund, 22185, Sweden

COMPLETED

Karolinska Institute

Stockholm, 112 81, Sweden

ACTIVE NOT RECRUITING

Karolinska Institute (Pediatric)

Stockholm, 171 77, Sweden

ACTIVE NOT RECRUITING

Inselspital Bern

Bern, 3010, Switzerland

RECRUITING

Hopitaux Universitaires de Geneve (HUG)

Geneva, 1205, Switzerland

RECRUITING

Centre Hopitalier Universitaire Vaudois

Lausanne, 1011, Switzerland

RECRUITING

Centre Hopitalier Universitaire Vaudois

Lausanne, 1011, Switzerland

RECRUITING

Kantonsspital St. Gallen

Sankt Gallen, 9007, Switzerland

RECRUITING

Klinik Hirslanden Zuerich

Zurich, 8032, Switzerland

RECRUITING

Royal Belfast Hospital for Sick Children

Belfast, BT12 6BE, United Kingdom

ACTIVE NOT RECRUITING

Birmingham Children's Hospital

Birmingham, B4 6NH, United Kingdom

ACTIVE NOT RECRUITING

University Hospitals Bristol and Weston

Bristol, BS2 8AE, United Kingdom

ACTIVE NOT RECRUITING

Addenbrooke's Hospital

Cambridge, CB2 2QQ, United Kingdom

ACTIVE NOT RECRUITING

University Hospital of Wales

Cardiff, CF14 4XW, United Kingdom

ACTIVE NOT RECRUITING

Western General Hospital

Edinburgh, EH4 2XU, United Kingdom

ACTIVE NOT RECRUITING

Royal Hospital for Sick Children and Young People

Edinburgh, EH9 1LF, United Kingdom

ACTIVE NOT RECRUITING

Gartnavel General Hospital

Glasgow, G12 0XH, United Kingdom

ACTIVE NOT RECRUITING

Queen Elizabeth University Hospital

Glasgow, G12 0YN, United Kingdom

ACTIVE NOT RECRUITING

Raigmore Hospital

Inverness, IV2 3UJ, United Kingdom

ACTIVE NOT RECRUITING

Leeds General Infirmary

Leeds, LS1 3EX, United Kingdom

ACTIVE NOT RECRUITING

Alder Hey Children's Hospital

Liverpool, L12 2AP, United Kingdom

ACTIVE NOT RECRUITING

Royal Liverpool University Hospital

Liverpool, L7 8XP, United Kingdom

ACTIVE NOT RECRUITING

National Hospital for Neurology and Neurosurgery

London, NW1 2PG, United Kingdom

ACTIVE NOT RECRUITING

Evelina Childrens Hospital

London, SE1 7EH, United Kingdom

ACTIVE NOT RECRUITING

Great Ormond Street Hospital for Children

London, WC1N 3JH, United Kingdom

ACTIVE NOT RECRUITING

Royal Manchester Children's Hospital

Manchester, M13 9WL, United Kingdom

ACTIVE NOT RECRUITING

Oxford University Hospital NHS Trust

Oxford, OX3 7LD, United Kingdom

ACTIVE NOT RECRUITING

Sheffield Childrens Hospital

Sheffield, S10 2RX, United Kingdom

ACTIVE NOT RECRUITING

Sheffield Teaching Hospitals

Sheffield, S5 7AU, United Kingdom

ACTIVE NOT RECRUITING

Southampton General Hospital

Southampton, SO16 6YD, United Kingdom

ACTIVE NOT RECRUITING

Stanmore Royal Orthopaedic Hospital

Stanmore, HA7 4LP, United Kingdom

ACTIVE NOT RECRUITING

Related Publications (2)

  • Carpenter TO, Fukumoto S, Haffner D, Imel EA, Ozono K, Ishii H, Li Z, Sandilands K, Joos-Vandewalle P, Lee C, Kanematsu M, McCullough KP, Brandi ML. Advancing Patient Evidence in XLH (APEX): Baseline analysis of a global data unification program. Bone. 2025 Dec;201:117649. doi: 10.1016/j.bone.2025.117649. Epub 2025 Sep 15.

  • Brandi ML, Ariceta G, Beck-Nielsen SS, Boot AM, Briot K, de Lucas Collantes C, Emma F, Giannini S, Haffner D, Keen R, Levtchenko E, Mӓkitie O, Nilsson O, Schnabel D, Tripto-Shkolnik L, Zillikens MC, Liu J, Tudor A, Mughal MZ. Post-authorisation safety study of burosumab use in paediatric, adolescent and adult patients with X-linked hypophosphataemia: rationale and description. Ther Adv Chronic Dis. 2022 Sep 5;13:20406223221117471. doi: 10.1177/20406223221117471. eCollection 2022.

MeSH Terms

Conditions

Familial Hypophosphatemic Rickets

Condition Hierarchy (Ancestors)

Rickets, HypophosphatemicRicketsBone Diseases, MetabolicBone DiseasesMusculoskeletal DiseasesHypophosphatemia, FamilialRenal Tubular Transport, Inborn ErrorsKidney DiseasesUrologic DiseasesFemale Urogenital DiseasesFemale Urogenital Diseases and Pregnancy ComplicationsUrogenital DiseasesMale Urogenital DiseasesMetal Metabolism, Inborn ErrorsMetabolism, Inborn ErrorsGenetic Diseases, InbornCongenital, Hereditary, and Neonatal Diseases and AbnormalitiesMetabolic DiseasesNutritional and Metabolic DiseasesCalcium Metabolism DisordersHypophosphatemiaPhosphorus Metabolism DisordersVitamin D DeficiencyAvitaminosisDeficiency DiseasesMalnutritionNutrition Disorders

Central Study Contacts

Study Design

Study Type
observational
Observational Model
OTHER
Time Perspective
OTHER
Target Duration
10 Years
Sponsor Type
INDUSTRY
Responsible Party
SPONSOR

Study Record Dates

First Submitted

June 13, 2017

First Posted

June 20, 2017

Study Start

September 12, 2017

Primary Completion (Estimated)

February 1, 2029

Study Completion (Estimated)

July 1, 2029

Last Updated

September 19, 2024

Record last verified: 2024-09

Locations