NCT01576523

Brief Summary

The aim of the study is to assess what happens to C1-esterase inhibitor that is administered under the skin of subjects with hereditary angioedema. Three different dosing regimens of C1-esterase inhibitor will be assessed. Each subject will be assigned to receive 2 of the 3 dosing regimens, each for 4 weeks. The activity and concentration of C1-esterase inhibitor in the blood will be measured during each 4-week period. The study will also examine how well C1-esterase inhibitor administered under the skin is tolerated by the subjects.

Trial Health

90
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
18

participants targeted

Target at P25-P50 for phase_1

Timeline
Completed

Started Apr 2012

Shorter than P25 for phase_1

Geographic Reach
2 countries

8 active sites

Status
completed

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Start

First participant enrolled

April 1, 2012

Completed
9 days until next milestone

First Submitted

Initial submission to the registry

April 10, 2012

Completed
2 days until next milestone

First Posted

Study publicly available on registry

April 12, 2012

Completed
8 months until next milestone

Primary Completion

Last participant's last visit for primary outcome

December 1, 2012

Completed
Same day until next milestone

Study Completion

Last participant's last visit for all outcomes

December 1, 2012

Completed
8.2 years until next milestone

Results Posted

Study results publicly available

February 1, 2021

Completed
Last Updated

February 1, 2021

Status Verified

January 1, 2021

Enrollment Period

8 months

First QC Date

April 10, 2012

Results QC Date

December 11, 2020

Last Update Submit

January 29, 2021

Conditions

Outcome Measures

Primary Outcomes (1)

  • Modeled C1-esterase Inhibitor Functional Activity Trough Level

    Mean trough C1-esterase inhibitor functional activity of the low, medium and high subcutaneous dose regimens, based on modeling and simulation

    at the fourth week of each dosing regimen

Secondary Outcomes (6)

  • As-observed C1-esterase Inhibitor Functional Activity Trough Level

    during the last week of 4-week dose regimen

  • C1-esterase Inhibitor Concentration Trough Level

    during the last week of 4-week dose regimen

  • C4 Concentration Trough Level

    during the last week of 4-week dose regimen

  • Change From Baseline in C1-esterase Inhibitor Functional Activity

    Baseline and during the last week of 4-week dose regimen

  • Change From Baseline in C1-esterase Inhibitor Concentration

    Baseline and during the last week of 4-week dose regimen

  • +1 more secondary outcomes

Study Arms (6)

Low, then medium, C1-esterase inhibitor dose

EXPERIMENTAL
Biological: C1-esterase inhibitor - single intravenous doseBiological: C1-esterase inhibitor - subcutaneous low doseBiological: C1-esterase inhibitor - subcutaneous medium dose

Medium, then low, C1-esterase inhibitor dose

EXPERIMENTAL
Biological: C1-esterase inhibitor - single intravenous doseBiological: C1-esterase inhibitor - subcutaneous low doseBiological: C1-esterase inhibitor - subcutaneous medium dose

Medium, then high, C1-esterase inhibitor dose

EXPERIMENTAL
Biological: C1-esterase inhibitor - single intravenous doseBiological: C1-esterase inhibitor - subcutaneous medium doseBiological: C1-esterase inhibitor - subcutaneous high dose

Low, then high, C1-esterase inhibitor dose

EXPERIMENTAL
Biological: C1-esterase inhibitor - single intravenous doseBiological: C1-esterase inhibitor - subcutaneous low doseBiological: C1-esterase inhibitor - subcutaneous high dose

High, then low, C1-esterase inhibitor dose

EXPERIMENTAL
Biological: C1-esterase inhibitor - single intravenous doseBiological: C1-esterase inhibitor - subcutaneous low doseBiological: C1-esterase inhibitor - subcutaneous high dose

High, then medium, C1-esterase inhibitor dose

EXPERIMENTAL
Biological: C1-esterase inhibitor - single intravenous doseBiological: C1-esterase inhibitor - subcutaneous medium doseBiological: C1-esterase inhibitor - subcutaneous high dose

Interventions

A single intravenous dose of C1-esterase inhibitor (Berinert) at 20 units per kg body weight will be administered to all subjects prior to receiving the first dose of subcutaneous C1-esterase inhibitor.

High, then low, C1-esterase inhibitor doseHigh, then medium, C1-esterase inhibitor doseLow, then high, C1-esterase inhibitor doseLow, then medium, C1-esterase inhibitor doseMedium, then high, C1-esterase inhibitor doseMedium, then low, C1-esterase inhibitor dose

A low dose of C1-esterase inhibitor will be administered subcutaneously twice a week for four weeks.

High, then low, C1-esterase inhibitor doseLow, then high, C1-esterase inhibitor doseLow, then medium, C1-esterase inhibitor doseMedium, then low, C1-esterase inhibitor dose

A medium dose of C1-esterase inhibitor will be administered subcutaneously twice a week for four weeks.

High, then medium, C1-esterase inhibitor doseLow, then medium, C1-esterase inhibitor doseMedium, then high, C1-esterase inhibitor doseMedium, then low, C1-esterase inhibitor dose

A high dose of C1-esterase inhibitor will administered subcutaneously twice a week for four weeks.

High, then low, C1-esterase inhibitor doseHigh, then medium, C1-esterase inhibitor doseLow, then high, C1-esterase inhibitor doseMedium, then high, C1-esterase inhibitor dose

Eligibility Criteria

Age18 Years+
Sexall
Healthy VolunteersNo
Age GroupsAdult (18-64), Older Adult (65+)

You may qualify if:

  • Males or females aged 18 years or older.
  • Laboratory-confirmed hereditary angioedema type I or II.
  • Less than two hereditary angioedema attacks per month in the last three months.
  • Body weight of 50.0 kg to 110.0 kg.

You may not qualify if:

  • Receiving prophylactic C1-esterase inhibitor therapy.
  • Received C1-esterase inhibitor, ecallantide, icatibant or any blood products for the prevention or treatment of hereditary angioedema within 7 days before the screening visit.
  • Intends to use recombinant C1-esterase inhibitor or fresh frozen plasma for the acute treatment of hereditary angioedema during the study.
  • Received androgen therapy (e.g., danazol, oxandrolone, stanozolol, testosterone) within 30 days before the screening visit.
  • Female subjects who started taking or changed dose of any hormonal contraceptive regimen or hormone replacement therapy (i.e., estrogen/progesterone-containing products) within 3 months prior to the screening visit.
  • Known or suspected hypersensitivity to the study product, or to any excipients of the study product.
  • Pregnancy or lactation.

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (8)

Study Site

Atlanta, Georgia, 30342, United States

Location

Study Site

Chevy Chase, Maryland, 20815, United States

Location

Study Site

Cincinnati, Ohio, 45231, United States

Location

Study Site

Toledo, Ohio, 43617, United States

Location

Study Site

Hershey, Pennsylvania, 19108, United States

Location

Study Site

Berlin, 10117, Germany

Location

Study Site

Frankfurt, 60596, Germany

Location

Study Site

Mainz, 55101, Germany

Location

Related Publications (1)

  • Zuraw BL, Cicardi M, Longhurst HJ, Bernstein JA, Li HH, Magerl M, Martinez-Saguer I, Rehman SM, Staubach P, Feuersenger H, Parasrampuria R, Sidhu J, Edelman J, Craig T. Phase II study results of a replacement therapy for hereditary angioedema with subcutaneous C1-inhibitor concentrate. Allergy. 2015 Oct;70(10):1319-28. doi: 10.1111/all.12658. Epub 2015 Aug 11.

MeSH Terms

Conditions

Hereditary Angioedema Types I and II

Condition Hierarchy (Ancestors)

Angioedemas, HereditaryAngioedemaVascular DiseasesCardiovascular DiseasesUrticariaSkin Diseases, VascularSkin DiseasesSkin and Connective Tissue DiseasesHypersensitivity, ImmediateHypersensitivityImmune System Diseases

Results Point of Contact

Title
Study Director
Organization
CSL Behring

Study Officials

  • Global Clinical Program Director

    CSL Behring

    STUDY DIRECTOR

Publication Agreements

PI is Sponsor Employee
No
Restriction Type
OTHER
Restrictive Agreement
Yes

Study Design

Study Type
interventional
Phase
phase 1
Allocation
NON RANDOMIZED
Masking
NONE
Purpose
PREVENTION
Intervention Model
CROSSOVER
Sponsor Type
INDUSTRY
Responsible Party
SPONSOR

Study Record Dates

First Submitted

April 10, 2012

First Posted

April 12, 2012

Study Start

April 1, 2012

Primary Completion

December 1, 2012

Study Completion

December 1, 2012

Last Updated

February 1, 2021

Results First Posted

February 1, 2021

Record last verified: 2021-01

Locations