NCT01528917

Brief Summary

This is a Natural History study to characterize key aspects of the clinical course of late onset Lysosomal Acid Lipase (LAL) Deficiency/ Cholesteryl Ester Storage Disease (CESD).

Trial Health

93
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
49

participants targeted

Target at P25-P50 for all trials

Timeline
Completed

Started Jun 2011

Geographic Reach
8 countries

16 active sites

Status
completed

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Start

First participant enrolled

June 1, 2011

Completed
8 months until next milestone

First Submitted

Initial submission to the registry

February 1, 2012

Completed
7 days until next milestone

First Posted

Study publicly available on registry

February 8, 2012

Completed
11 months until next milestone

Primary Completion

Last participant's last visit for primary outcome

January 1, 2013

Completed
4 months until next milestone

Study Completion

Last participant's last visit for all outcomes

May 1, 2013

Completed
Last Updated

July 20, 2016

Status Verified

April 1, 2013

Enrollment Period

1.6 years

First QC Date

February 1, 2012

Last Update Submit

July 19, 2016

Conditions

Keywords

Lysosomal Storage DiseaseLate Onset Lysosomal Acid Lipase (LAL) DeficiencyAcid cholesteryl ester hydrolase deficiency, type 2Acid lipase diseaseCholesterol ester hydrolase deficiencyLAL DeficiencyLIPA DeficiencyWolman disease

Outcome Measures

Primary Outcomes (1)

  • Clinical History Summary

    Characterize patient demographic data and clinical course of disease using descriptive statistics.

    Expected average of 15 years

Eligibility Criteria

Age5 Years+
Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)
Sampling MethodNon-Probability Sample
Study Population

Patients diagnosed with late onset LAL Deficiency/ Cholesteryl Ester Storage Disease (CESD).

You may qualify if:

  • Patients with late onset LAL Deficiency/ Cholesteryl Ester Storage Disease (CESD) who are 5 years of age or older and have required data points in their medical record

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (16)

Stanford University

Stanford, California, 94305, United States

Location

Children's Memorial Hospital

Chicago, Illinois, 60614, United States

Location

University of Minnesota

Minneapolis, Minnesota, 55455, United States

Location

Morgan Stanley Children's Hospital of New York-Presbyterian

New York, New York, 10032, United States

Location

Children's Hospital of Pittsburgh

Pittsburgh, Pennsylvania, 15224, United States

Location

Seattle Children's

Seattle, Washington, 98105, United States

Location

Hospital for Sick Kids

Toronto, Canada

Location

1st Faculty of Medicine Charles University

Prague, Czechia

Location

Hôpital Necker-Enfants Malades

Paris, France

Location

Gaslini Institute

Genoa, Italy

Location

Regina Margherita Hospital

Turin, Italy

Location

Children's Memorial Health Institute

Warsaw, Poland

Location

Hopitaux Universitares De Geneve

Geneva, Switzerland

Location

Birmingham Children's Hospital

Birmingham, United Kingdom

Location

Addenbrooke's Hospital

Cambridge, United Kingdom

Location

Salford Royal

Salford, United Kingdom

Location

Related Publications (2)

  • Burton BK, Silliman N, Marulkar S. Progression of liver disease in children and adults with lysosomal acid lipase deficiency. Curr Med Res Opin. 2017 Jul;33(7):1211-1214. doi: 10.1080/03007995.2017.1309371. Epub 2017 Apr 3.

  • Burton BK, Deegan PB, Enns GM, Guardamagna O, Horslen S, Hovingh GK, Lobritto SJ, Malinova V, McLin VA, Raiman J, Di Rocco M, Santra S, Sharma R, Sykut-Cegielska J, Whitley CB, Eckert S, Valayannopoulos V, Quinn AG. Clinical Features of Lysosomal Acid Lipase Deficiency. J Pediatr Gastroenterol Nutr. 2015 Dec;61(6):619-25. doi: 10.1097/MPG.0000000000000935.

Related Links

MeSH Terms

Conditions

Cholesterol Ester Storage DiseaseWolman DiseaseLysosomal Storage Diseases

Condition Hierarchy (Ancestors)

LipidosesLipid Metabolism, Inborn ErrorsMetabolism, Inborn ErrorsGenetic Diseases, InbornCongenital, Hereditary, and Neonatal Diseases and AbnormalitiesLipid Metabolism DisordersMetabolic DiseasesNutritional and Metabolic DiseasesInfant, Newborn, Diseases

Study Design

Study Type
observational
Observational Model
COHORT
Time Perspective
RETROSPECTIVE
Sponsor Type
INDUSTRY
Responsible Party
SPONSOR

Study Record Dates

First Submitted

February 1, 2012

First Posted

February 8, 2012

Study Start

June 1, 2011

Primary Completion

January 1, 2013

Study Completion

May 1, 2013

Last Updated

July 20, 2016

Record last verified: 2013-04

Data Sharing

IPD Sharing
Will not share

Locations