NCT04808505

Brief Summary

This is a Phase 3, open-label, multicenter study to evaluate the safety, efficacy, PK, PD, and immunogenicity of cipaglucosidase alfa/miglustat treatment in ERT-experienced and ERT-naïve pediatric subjects with IOPD.

Trial Health

83
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
36

participants targeted

Target at below P25 for phase_3

Timeline
14mo left

Started Jul 2023

Typical duration for phase_3

Geographic Reach
6 countries

14 active sites

Status
recruiting

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Progress71%
Jul 2023Jul 2027

First Submitted

Initial submission to the registry

March 10, 2021

Completed
12 days until next milestone

First Posted

Study publicly available on registry

March 22, 2021

Completed
2.3 years until next milestone

Study Start

First participant enrolled

July 18, 2023

Completed
4 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

July 1, 2027

Expected
Same day until next milestone

Study Completion

Last participant's last visit for all outcomes

July 1, 2027

Last Updated

January 22, 2026

Status Verified

January 1, 2026

Enrollment Period

4 years

First QC Date

March 10, 2021

Last Update Submit

January 20, 2026

Conditions

Outcome Measures

Primary Outcomes (1)

  • Proportion of subjects with infusion-associated reactions (IARs)

    104 weeks

Study Arms (2)

Cohort 1: Cipaglucosidase Alfa/Miglustat in ERT-experienced pediatric IOPD subjects

EXPERIMENTAL

Pediatric IOPD subjects 6 months to \<18 years experiencing clinical decline

Biological: Cipaglucosidase alfaDrug: Miglustat

Cohort 2: Cipaglucosidase Alfa/Miglustat in ERT-naïve pediatric IOPD subjects

EXPERIMENTAL

Pediatric IOPD subjects \<6 months

Biological: Cipaglucosidase alfaDrug: Miglustat

Interventions

Sterile lyophilized powder intravenous (IV) infusion

Also known as: ATB200
Cohort 1: Cipaglucosidase Alfa/Miglustat in ERT-experienced pediatric IOPD subjectsCohort 2: Cipaglucosidase Alfa/Miglustat in ERT-naïve pediatric IOPD subjects

65 mg oral capsules

Also known as: AT2221
Cohort 1: Cipaglucosidase Alfa/Miglustat in ERT-experienced pediatric IOPD subjectsCohort 2: Cipaglucosidase Alfa/Miglustat in ERT-naïve pediatric IOPD subjects

Eligibility Criteria

AgeUp to 17 Years
Sexall
Healthy VolunteersNo
Age GroupsChild (0-17)

You may qualify if:

  • Cohort 1:
  • Male or female subjects who are aged 6 months to \< 18 years on Day 1
  • Subject must have documentation of IOPD genotype
  • Subject must have had hypertrophic cardiomyopathy at the time of diagnosis
  • Subject must have received ERT for at least 6 months immediately before enrollment. For subjects whose ERT dosage has been modified, the subject must have been on the modified dosage and regimen for at least 3 months before enrollment
  • Subjects aged ≥ 12 to \< 18 years must perform one valid 6-minute walk test (6MWT) (≥ 75 meters) at screening; Subjects aged ≥ 5 to \< 12 years must perform one valid 6MWT (≥ 40 meters) at screening; Subjects aged 18 months to \< 5 years must be ambulatory and assessed to be likely to be able to perform 6MWT (≥ 40 meters) when they turn 5 years old
  • Subjects must have experienced a clinical decline on their current rhGAA dose and frequency
  • Cohort 2:
  • Male or female subjects who are aged 0 to \<6 months at Day 1
  • Subject must have documentation of IOPD genotype
  • Subject must have had hypertrophic cardiomyopathy at the time of diagnosis
  • Subject is ERT-naïve
  • Long-term Extension (Cohort 1 or Cohort 2):
  • \. Subject must have, in the opinion of the investigator, benefited from therapy with cipaglucosidase alfa/miglustat during the 104-week primary treatment period with no significant safety concerns.

You may not qualify if:

  • Cohort 1 and Cohort 2, unless specified
  • Subject requires invasive ventilation (eg, tracheostomy)
  • Subject is CRIM negative and has not received prophylactic immunomodulation (Cohort 1); Subject is CRIM negative and will not be receiving prophylactic immunomodulation (Cohort 2)
  • Subject has a history of life-threatening IARs/hypersensitivity (eg, anaphylaxis and severe cutaneous reactions) to ERT (eg, alglucosidase alfa, cipaglucosidase alfa, miglustat) or other iminosugars, or to any of the excipients, where rechallenge was unsuccessful
  • Subject has prior history of illness or condition known to affect motor function
  • Female subject is pregnant (or intends to get pregnant) or breastfeeding at screening (Cohort 1)

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (14)

University of Florida Clinical Research Center

Gainesville, Florida, 32610, United States

RECRUITING

The Emory Clinic

Atlanta, Georgia, 30322, United States

RECRUITING

Duke University Early Phase Research Unit

Durham, North Carolina, 27710, United States

RECRUITING

Cincinnati Children's Hospital Medical Center

Cincinnati, Ohio, 54229, United States

RECRUITING

UPMC Hospital of Pittsburgh

Pittsburgh, Pennsylvania, 15224, United States

RECRUITING

University of Utah, Clinical and Translational Sciences Institute

Salt Lake City, Utah, 84108, United States

RECRUITING

Universitätsklinikum Gießen und Marburg GmbH, Zentrum fur Kinderheilkunde und Jugendmedizin Abteilung fur Kinderneurologic, Sozialpadiatric und Epileptologie

Giessen, 35392, Germany

RECRUITING

Universitätsklinikum Heidelberg - Pädiatrisches Klinisch-Pharmakologisches Studienzentrum (paedKliPS)

Heidelberg, 69120, Germany

RECRUITING

SphinCS GmbH

Höchheim, 65239, Germany

RECRUITING

Universitätsklinikum Münster Klinik für Kinder- und Jugendmedizin Albert-Schweitzer-Campus 1

Münster, 48149, Germany

RECRUITING

AOU Federico II

Naples, 80131, Italy

RECRUITING

Erasmus MC, Sophia Kinderziekenhuis

Rotterdam, 3015 GD, Netherlands

RECRUITING

National Taiwan University Hospital

Taipei, 100, Taiwan

WITHDRAWN

Great Ormond Street Hospital for Children NHS Foundation Trust

London, WC1N3JH, United Kingdom

RECRUITING

MeSH Terms

Interventions

miglustat

Central Study Contacts

Study Design

Study Type
interventional
Phase
phase 3
Allocation
NON RANDOMIZED
Masking
NONE
Purpose
TREATMENT
Intervention Model
PARALLEL
Sponsor Type
INDUSTRY
Responsible Party
SPONSOR
Expanded Access
Yes

Study Record Dates

First Submitted

March 10, 2021

First Posted

March 22, 2021

Study Start

July 18, 2023

Primary Completion (Estimated)

July 1, 2027

Study Completion (Estimated)

July 1, 2027

Last Updated

January 22, 2026

Record last verified: 2026-01

Data Sharing

IPD Sharing
Will not share

Locations