NCT04531189

Brief Summary

The primary objective of the study is to determine the relevance and appropriateness of outcome assessments, including biomarkers, within the Wilson disease population to inform study design and endpoint selection for future clinical studies.

Trial Health

90
On Track

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Enrollment
16

participants targeted

Target at below P25 for all trials

Timeline
Completed

Started Dec 2020

Geographic Reach
2 countries

6 active sites

Status
completed

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

First Submitted

Initial submission to the registry

July 27, 2020

Completed
1 month until next milestone

First Posted

Study publicly available on registry

August 28, 2020

Completed
4 months until next milestone

Study Start

First participant enrolled

December 11, 2020

Completed
1.3 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

March 25, 2022

Completed
Same day until next milestone

Study Completion

Last participant's last visit for all outcomes

March 25, 2022

Completed
Last Updated

April 29, 2022

Status Verified

April 1, 2022

Enrollment Period

1.3 years

First QC Date

July 27, 2020

Last Update Submit

April 28, 2022

Conditions

Outcome Measures

Primary Outcomes (8)

  • Clinical manifestation of Wilson Disease under study: demographics

    30 days

  • Clinical manifestation of Wilson Disease under study: general medical history, Wilson Disease history and treatments

    30 days

  • Clinical manifestation of Wilson Disease under study: patient reported outcomes and clinician reported outcomes

    30 days

  • Clinical manifestation of Wilson Disease under study: activity monitoring

    30 days

  • Clinical manifestation of Wilson Disease under study: motor function

    30 days

  • Clinical manifestation of Wilson Disease under study: joint pain

    30 days

  • Clinical manifestation of Wilson Disease under study: serum copper biomarker assessments

    30 days

  • Clinical manifestation of Wilson Disease under study: 24-hour urinary copper concentration

    30 days

Eligibility Criteria

Age12 Years+
Sexall
Healthy VolunteersNo
Age GroupsChild (0-17), Adult (18-64), Older Adult (65+)
Sampling MethodNon-Probability Sample
Study Population

Subjects with a confirmed diagnosis of Wilson Disease will be enrolled from outpatient clinics and metabolic genetic centers in the United States. Subjects may participate regardless of their current treatment. Subjects who have had a liver transplant for treatment of Wilson Disease are also invited to participate.

You may qualify if:

  • Male or female ≥ 12 years of age at the time written informed consent is provided.
  • Confirmed diagnosis of Wilson disease.
  • Have a documented history of copper chelator (ie, penicillamine, trientine) and/or zinc therapy or be ≥ 1 year post liver transplant with no active associated complications.
  • Willing and able to comply with all study procedures and requirements. If \< 18 years of age (or as required by region), have a caregiver who is willing and able to assist with study requirements if needed.
  • Willing and able to provide written informed consent after the study has been explained and before any study-related data are collected or study-related procedures are performed. If \< 18 years of age (or as required by region), willing and able to provide written assent and have a legally authorized representative who is willing and able to provide written informed consent after the study has been explained and before any study-related data are collected or study-related procedures are performed.

You may not qualify if:

  • History of liver disease due to a medical condition unrelated to Wilson disease.
  • Liver fibrosis stage F3 or F4.
  • Decompensated hepatic cirrhosis and/or evidence of portal hypertension.
  • Marked neurological disease requiring either nasogastric feeding or intensive inpatient medical care.
  • Female subject who is pregnant or breastfeeding or who plans to become pregnant at any time during the study.
  • Female subject of childbearing potential who has a positive urine pregnancy test on Day 1 or is unwilling to have additional pregnancy tests during the study.
  • Current or previous participation in a gene transfer study.
  • Presence or history of any disease or condition that, in the Investigator's opinion, would interfere with the subject's safety or ability to participate in the study or significantly affect interpretation of study results.

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (6)

Yale University School of Medicine

New Haven, Connecticut, 06510, United States

Location

Jackson Memorial Hospital Miami Transplant Unit University of Miami Miller School of Medicine

Miami, Florida, 33136, United States

Location

Northwestern University Feinberg School of Medicine

Chicago, Illinois, 60611, United States

Location

University of Michigan Michigan Medicine Hepatology Clinic Taubman Center

Ann Arbor, Michigan, 48109, United States

Location

Seattle Children's Hospital

Seattle, Washington, 98105, United States

Location

Universitätsklinikum Heidelberg

Heidelberg, Baden-Wurttemberg, 69120, Germany

Location

Related Links

Biospecimen

Retention: SAMPLES WITH DNA

Whole blood sample for future UX701 related research (DNA, RNA, proteins)

MeSH Terms

Conditions

Hepatolenticular Degeneration

Condition Hierarchy (Ancestors)

Liver DiseasesDigestive System DiseasesBasal Ganglia DiseasesBrain DiseasesCentral Nervous System DiseasesNervous System DiseasesBrain Diseases, Metabolic, InbornBrain Diseases, MetabolicMovement DisordersHeredodegenerative Disorders, Nervous SystemNeurodegenerative DiseasesGenetic Diseases, InbornCongenital, Hereditary, and Neonatal Diseases and AbnormalitiesMetabolism, Inborn ErrorsMetal Metabolism, Inborn ErrorsMetabolic DiseasesNutritional and Metabolic Diseases

Study Officials

  • Ultragenyx Medical Director

    Ultragenyx Pharmaceutical

    STUDY DIRECTOR

Study Design

Study Type
observational
Observational Model
COHORT
Time Perspective
PROSPECTIVE
Sponsor Type
INDUSTRY
Responsible Party
SPONSOR

Study Record Dates

First Submitted

July 27, 2020

First Posted

August 28, 2020

Study Start

December 11, 2020

Primary Completion

March 25, 2022

Study Completion

March 25, 2022

Last Updated

April 29, 2022

Record last verified: 2022-04

Data Sharing

IPD Sharing
Will not share

Locations