NCT02148900

Brief Summary

The objective of this study is to determine whether a simple blood test can be a useful clinical tool for monitoring aortic disease in Marfan syndrome and Marfan-related disorders.

Trial Health

43
At Risk

Trial Health Score

Automated assessment based on enrollment pace, timeline, and geographic reach

Trial has exceeded expected completion date
Enrollment
336

participants targeted

Target at P75+ for all trials

Timeline
Completed

Started May 2013

Longer than P75 for all trials

Geographic Reach
1 country

5 active sites

Status
unknown

Health score is calculated from publicly available data and should be used for screening purposes only.

Trial Relationships

Click on a node to explore related trials.

Study Timeline

Key milestones and dates

Study Start

First participant enrolled

May 1, 2013

Completed
1.1 years until next milestone

First Submitted

Initial submission to the registry

May 23, 2014

Completed
5 days until next milestone

First Posted

Study publicly available on registry

May 28, 2014

Completed
3.5 years until next milestone

Primary Completion

Last participant's last visit for primary outcome

December 1, 2017

Completed
Same day until next milestone

Study Completion

Last participant's last visit for all outcomes

December 1, 2017

Completed
Last Updated

January 5, 2017

Status Verified

January 1, 2017

Enrollment Period

4.6 years

First QC Date

May 23, 2014

Last Update Submit

January 4, 2017

Conditions

Keywords

Marfan syndromeblood testaortic root sizeMarfan related disorders

Outcome Measures

Primary Outcomes (1)

  • microfibril fragments

    Plasma will be tested using sandwich ELISAs and standard curves to quantitate fragments of fibrillin-1, fibrillin-2, and fibulin-4.

    measured yearly over 5 years

Secondary Outcomes (1)

  • Aortic root growth

    yearly for five years

Other Outcomes (1)

  • medical and lifestyle issues

    yearly for five years

Study Arms (3)

Marfan

Diagnosis of Marfan syndrome, according to Ghent criteria.

Marfan Related Disorders

Diagnosis of Loeys-Dietz syndrome, vascular Ehlers-Danlos syndrome, or Familial Thoracic Aortic Aneurysm and Dissection.

Control Subjects

Unaffected by Marfan or Marfan related disorders.

Eligibility Criteria

Age4 Years - 26 Years
Sexall
Healthy VolunteersYes
Age GroupsChild (0-17), Adult (18-64)
Sampling MethodProbability Sample
Study Population

The study population includes 3 groups: (1) individuals with Marfan syndrome; (2) individuals with Marfan-related disorders; (3) unaffected controls. Both genders, ages 4 to 26, will be included. Geographic locations will include the Pacific Northwest, Texas, and the Salt Lake City/Denver areas.

You may qualify if:

  • Age 4-26 years of age for all participants
  • Able and willing to sign informed consent/assent
  • Signed HIPPA compliant research authorization

You may not qualify if:

  • Other known cardiovascular disorder for unaffected controls

Contact the study team to confirm eligibility.

Sponsors & Collaborators

Study Sites (5)

Lurie Childrens Hospital

Chicago, Illinois, 60611-2605, United States

RECRUITING

University of Nebraska

Omaha, Nebraska, 68114, United States

RECRUITING

Oregon Health & Science University

Portland, Oregon, 97239, United States

RECRUITING

Shriners Hospital for Children

Portland, Oregon, 97239, United States

RECRUITING

University of Texas at Houston

Houston, Texas, 77030, United States

RECRUITING

Biospecimen

Retention: SAMPLES WITH DNA

Plasma Frozen Cells

MeSH Terms

Conditions

Marfan Syndrome

Condition Hierarchy (Ancestors)

Bone Diseases, DevelopmentalBone DiseasesMusculoskeletal DiseasesHeart Defects, CongenitalCardiovascular AbnormalitiesCardiovascular DiseasesHeart DiseasesAbnormalities, MultipleCongenital AbnormalitiesCongenital, Hereditary, and Neonatal Diseases and AbnormalitiesGenetic Diseases, InbornConnective Tissue DiseasesSkin and Connective Tissue Diseases

Study Officials

  • Lynn Y. Sakai, Ph.D.

    Shriners Hospitals for Children

    PRINCIPAL INVESTIGATOR

Central Study Contacts

Lynn Y. Sakai, Ph.D.

CONTACT

Susan Sienko, Ph.D.

CONTACT

Study Design

Study Type
observational
Observational Model
CASE CONTROL
Time Perspective
PROSPECTIVE
Target Duration
5 Years
Sponsor Type
OTHER
Responsible Party
PRINCIPAL INVESTIGATOR
PI Title
Sr. Investigator

Study Record Dates

First Submitted

May 23, 2014

First Posted

May 28, 2014

Study Start

May 1, 2013

Primary Completion

December 1, 2017

Study Completion

December 1, 2017

Last Updated

January 5, 2017

Record last verified: 2017-01

Data Sharing

IPD Sharing
Will not share

Locations